急性播散性胰膜炎与α -1抗胰蛋白酶缺乏相关。

IF 0.9 Q4 DERMATOLOGY Case Reports in Dermatology Pub Date : 2022-09-01 DOI:10.1159/000526156
António Guilherme Murinello, Helena Sá Damásio, Pedro Guedes, António Manuel de Figueiredo, Adriana Santos, Ana Serrano
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引用次数: 0

摘要

α -1抗胰蛋白酶缺乏症虽然是最常见的遗传性疾病之一,但却是一种非常罕见且经常无法诊断的pannicultis病因。作者提出了一个病例的特点是急性累及几个区域在胸部,腹部和四肢,发生在会阴区反复创伤引起的长时间的循环。在进行鉴别诊断和确定病因后,患者开始接受血浆来源的合成人α -1蛋白酶抑制剂的强化治疗,此后病情得到控制。我们建议终生使用这种药物。在10年随访结束时,没有发现肺气肿或肝脏疾病的证据。作者执行一个简明的审查遗传和致病机制背后的这种疾病,特别侧重于泛膜炎及其治疗。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

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Acute Disseminated Panniculitis Associated with Alpha-1 Antitrypsin Deficiency.

Alpha-1 antitrypsin deficiency, although one of the most common genetic diseases, is a very rare and often undiagnosed cause of panniculitis. The authors present a case characterized by an acute involvement of several areas in the thorax, abdomen, and limbs, occurring after repetitive trauma of the perineal area caused by a long period of cycling. After performing the differential diagnosis and establishing etiology, the patient was started on augmentation therapy with plasma-derived synthetic human alpha-1 proteinase inhibitor and the disease has been under control since then. We recommend lifelong treatment with this medication. At the end of a 10-year follow-up, there has been no evidence of pulmonary emphysema or liver disease. The authors perform a concise review of the genetic and pathogenic mechanisms behind this disease, with a special focus on panniculitis and its treatment.

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CiteScore
1.60
自引率
0.00%
发文量
57
审稿时长
9 weeks
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