Wilms 肿瘤伴有血清甲胎蛋白升高:凸显对新型循环生物标志物的需求

IF 1.3 4区 医学 Q3 PATHOLOGY Pediatric and Developmental Pathology Pub Date : 2024-05-01 Epub Date: 2023-12-14 DOI:10.1177/10935266231213467
Rebecca Green, Adeeb Ahmed, Ben Fleming, Anna-May Long, Sam Behjati, Jamie Trotman, Patrick Tarpey, James C Nicholson, Nicholas Coleman, C Elizabeth Hook, Matthew J Murray
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引用次数: 0

摘要

Wilms瘤(WT)是儿童肾癌最常见的病因。在欧洲,大多数病例都是在术前化疗前根据典型的临床和放射学检查结果确诊的。在这里,我们描述了一例小男孩腹部巨大肿瘤的病例,确诊时血清甲胎蛋白(AFP)水平升高。鉴于肿瘤的非典型特征,患者接受了活检,组织学检查结果与WT一致,显示为三相WT,存在上皮、基质和胚芽元素,WT1和CD56免疫组化染色阳性。在术前化疗期间,尽管出现了放射学反应,但连续的血清甲胎蛋白测量结果显示甲胎蛋白进一步升高,随后在肾切除术后降至正常值。切除标本中的基质和上皮细胞分别占 55% 和 45%,无增生,但使用 AFP 染色的免疫组化显示粘液性肠上皮呈阳性,与血清 AFP 观察结果一致。该病例的肿瘤反应与血清 AFP 水平之间缺乏相关性,这凸显了临床上对确定 WT 特异性循环肿瘤标志物的普遍需求。
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Wilms Tumor With Raised Serum Alpha-Fetoprotein: Highlighting the Need for Novel Circulating Biomarkers.

Wilms tumor (WT) is the commonest cause of renal cancer in children. In Europe, a diagnosis is made for most cases on typical clinical and radiological findings, prior to pre-operative chemotherapy. Here, we describe a case of a young boy presenting with a large abdominal tumor, associated with raised serum alpha-fetoprotein (AFP) levels at diagnosis. Given the atypical features present, a biopsy was taken, and histology was consistent with WT, showing triphasic WT, with epithelial, stromal, and blastemal elements present, and positive WT1 and CD56 immunohistochemical staining. During pre-operative chemotherapy, serial serum AFP measurements showed further increases, despite a radiological response, before a subsequent fall to normal following nephrectomy. The resection specimen was comprised of ~55% and ~45% stromal and epithelial elements, respectively, with no anaplasia, but immunohistochemistry using AFP staining revealed positive mucinous intestinal epithelium, consistent with the serum AFP observations. The lack of correlation between tumor response and serum AFP levels in this case highlights a more general clinical unmet need to identify WT-specific circulating tumor markers.

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来源期刊
CiteScore
3.70
自引率
5.30%
发文量
59
审稿时长
6-12 weeks
期刊介绍: The Journal covers the spectrum of disorders of early development (including embryology, placentology, and teratology), gestational and perinatal diseases, and all diseases of childhood. Studies may be in any field of experimental, anatomic, or clinical pathology, including molecular pathology. Case reports are published only if they provide new insights into disease mechanisms or new information.
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