对一名患者从增生发展为子宫内膜癌12年的深层分子追踪。

IF 1.8 Q3 MEDICINE, RESEARCH & EXPERIMENTAL Cold Spring Harbor Molecular Case Studies Pub Date : 2024-01-10 Print Date: 2023-12-01 DOI:10.1101/mcs.a006311
Katherine Reid, Olga Camacho-Vanegas, Deep Pandya, Sandra Catalina Camacho, Rui Fang Qiao, Tamara Kalir, Maria M Padron-Rhenals, Ann-Marie Beddoe, Peter Dottino, John A Martignetti
{"title":"对一名患者从增生发展为子宫内膜癌12年的深层分子追踪。","authors":"Katherine Reid, Olga Camacho-Vanegas, Deep Pandya, Sandra Catalina Camacho, Rui Fang Qiao, Tamara Kalir, Maria M Padron-Rhenals, Ann-Marie Beddoe, Peter Dottino, John A Martignetti","doi":"10.1101/mcs.a006311","DOIUrl":null,"url":null,"abstract":"<p><p>Although the progressive histologic steps leading to endometrial cancer (EndoCA), the most common female reproductive tract malignancy, from endometrial hyperplasia are well-established, the molecular changes accompanying this malignant transformation in a single patient have never been described. We had the unique opportunity to investigate the paired histologic and molecular features associated with the 12-yr development of EndoCA in a postmenopausal female who could not undergo hysterectomy and instead underwent progesterone treatment. Using a specially designed 58-gene next-generation sequencing panel, we analyzed a total of 10 sequential biopsy samples collected over this time frame. A total of eight pathogenic/likely pathogenic mutations in seven genes, <i>APC</i>, <i>ARID1A</i>, <i>CTNNB1</i>, <i>CDKN2A</i>, <i>KRAS</i>, <i>PTEN</i>, and <i>TP53</i>, were identified. A <i>PTEN</i> nonsense mutation p.W111* was present in all samples analyzed except histologically normal endometrium. Apart from this <i>PTEN</i> mutation, the only other recurrent mutation was <i>KRAS</i> G12D, which was present in six biopsy samplings, including histologically normal tissue obtained at the patient's first visit but not detectable in the cancer. The <i>PTEN</i> p.W111* mutant allele fractions were lowest in benign, inactive endometrial glands (0.7%), highest in adenocarcinoma (36.9%), and, notably, were always markedly reduced following progesterone treatment. To our knowledge, this report provides the first molecular characterization of EndoCA development in a single patient. A single <i>PTEN</i> mutation was present throughout the 12 years of cancer development. Importantly, and with potential significance toward medical and nonsurgical management of EndoCA, progesterone treatments were consistently noted to markedly decrease <i>PTEN</i> mutant allele fractions to precancerous levels.</p>","PeriodicalId":10360,"journal":{"name":"Cold Spring Harbor Molecular Case Studies","volume":null,"pages":null},"PeriodicalIF":1.8000,"publicationDate":"2024-01-10","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10815295/pdf/","citationCount":"0","resultStr":"{\"title\":\"Deep molecular tracking over the 12-yr development of endometrial cancer from hyperplasia in a single patient.\",\"authors\":\"Katherine Reid, Olga Camacho-Vanegas, Deep Pandya, Sandra Catalina Camacho, Rui Fang Qiao, Tamara Kalir, Maria M Padron-Rhenals, Ann-Marie Beddoe, Peter Dottino, John A Martignetti\",\"doi\":\"10.1101/mcs.a006311\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<p><p>Although the progressive histologic steps leading to endometrial cancer (EndoCA), the most common female reproductive tract malignancy, from endometrial hyperplasia are well-established, the molecular changes accompanying this malignant transformation in a single patient have never been described. We had the unique opportunity to investigate the paired histologic and molecular features associated with the 12-yr development of EndoCA in a postmenopausal female who could not undergo hysterectomy and instead underwent progesterone treatment. Using a specially designed 58-gene next-generation sequencing panel, we analyzed a total of 10 sequential biopsy samples collected over this time frame. A total of eight pathogenic/likely pathogenic mutations in seven genes, <i>APC</i>, <i>ARID1A</i>, <i>CTNNB1</i>, <i>CDKN2A</i>, <i>KRAS</i>, <i>PTEN</i>, and <i>TP53</i>, were identified. A <i>PTEN</i> nonsense mutation p.W111* was present in all samples analyzed except histologically normal endometrium. Apart from this <i>PTEN</i> mutation, the only other recurrent mutation was <i>KRAS</i> G12D, which was present in six biopsy samplings, including histologically normal tissue obtained at the patient's first visit but not detectable in the cancer. The <i>PTEN</i> p.W111* mutant allele fractions were lowest in benign, inactive endometrial glands (0.7%), highest in adenocarcinoma (36.9%), and, notably, were always markedly reduced following progesterone treatment. To our knowledge, this report provides the first molecular characterization of EndoCA development in a single patient. A single <i>PTEN</i> mutation was present throughout the 12 years of cancer development. Importantly, and with potential significance toward medical and nonsurgical management of EndoCA, progesterone treatments were consistently noted to markedly decrease <i>PTEN</i> mutant allele fractions to precancerous levels.</p>\",\"PeriodicalId\":10360,\"journal\":{\"name\":\"Cold Spring Harbor Molecular Case Studies\",\"volume\":null,\"pages\":null},\"PeriodicalIF\":1.8000,\"publicationDate\":\"2024-01-10\",\"publicationTypes\":\"Journal Article\",\"fieldsOfStudy\":null,\"isOpenAccess\":false,\"openAccessPdf\":\"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10815295/pdf/\",\"citationCount\":\"0\",\"resultStr\":null,\"platform\":\"Semanticscholar\",\"paperid\":null,\"PeriodicalName\":\"Cold Spring Harbor Molecular Case Studies\",\"FirstCategoryId\":\"1085\",\"ListUrlMain\":\"https://doi.org/10.1101/mcs.a006311\",\"RegionNum\":0,\"RegionCategory\":null,\"ArticlePicture\":[],\"TitleCN\":null,\"AbstractTextCN\":null,\"PMCID\":null,\"EPubDate\":\"2023/12/1 0:00:00\",\"PubModel\":\"Print\",\"JCR\":\"Q3\",\"JCRName\":\"MEDICINE, RESEARCH & EXPERIMENTAL\",\"Score\":null,\"Total\":0}","platform":"Semanticscholar","paperid":null,"PeriodicalName":"Cold Spring Harbor Molecular Case Studies","FirstCategoryId":"1085","ListUrlMain":"https://doi.org/10.1101/mcs.a006311","RegionNum":0,"RegionCategory":null,"ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":null,"EPubDate":"2023/12/1 0:00:00","PubModel":"Print","JCR":"Q3","JCRName":"MEDICINE, RESEARCH & EXPERIMENTAL","Score":null,"Total":0}
引用次数: 0

摘要

虽然子宫内膜增生导致子宫内膜癌症(EndoCA)(最常见的女性生殖道恶性肿瘤)的渐进性组织学步骤已经确定,但从未描述过单个患者伴随这种恶性转化的分子变化。我们有一个独特的机会来研究与绝经后女性EndoCA 12年发展相关的配对组织学和分子特征,这些女性不能进行子宫切除术,而是接受了孕酮治疗。使用专门设计的58个基因的下一代测序面板,我们分析了在这段时间内收集的总共10个顺序活检样本。在APC、ARID1A、CTNNB1、CDKN2A、KRAS、PTEN和TP53七个基因中,共鉴定出八个致病性/可能致病性突变。除组织学正常的子宫内膜外,所有分析样本中均存在PTEN无义突变p.W111*。除此PTEN突变外,唯一的其他复发性突变是KRAS G12D;存在于四个活检样本中,包括患者首次就诊时获得的组织学正常组织,但在癌症中未检测到。PTEN p.W111*突变等位基因组分在良性、不活动的子宫内膜腺中最低(0.7%),在腺癌中最高(36.9%),值得注意的是,在孕酮治疗后总是显著降低。据我们所知,本报告首次提供了单个患者EndoCA发展的分子特征。在癌症发展的12年中,单个PTEN突变存在。重要的是,黄体酮治疗对EndoCA的医学和非手术治疗具有潜在意义,一直被注意到能显著降低PTEN突变等位基因组分至癌前水平。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
查看原文
分享 分享
微信好友 朋友圈 QQ好友 复制链接
本刊更多论文
Deep molecular tracking over the 12-yr development of endometrial cancer from hyperplasia in a single patient.

Although the progressive histologic steps leading to endometrial cancer (EndoCA), the most common female reproductive tract malignancy, from endometrial hyperplasia are well-established, the molecular changes accompanying this malignant transformation in a single patient have never been described. We had the unique opportunity to investigate the paired histologic and molecular features associated with the 12-yr development of EndoCA in a postmenopausal female who could not undergo hysterectomy and instead underwent progesterone treatment. Using a specially designed 58-gene next-generation sequencing panel, we analyzed a total of 10 sequential biopsy samples collected over this time frame. A total of eight pathogenic/likely pathogenic mutations in seven genes, APC, ARID1A, CTNNB1, CDKN2A, KRAS, PTEN, and TP53, were identified. A PTEN nonsense mutation p.W111* was present in all samples analyzed except histologically normal endometrium. Apart from this PTEN mutation, the only other recurrent mutation was KRAS G12D, which was present in six biopsy samplings, including histologically normal tissue obtained at the patient's first visit but not detectable in the cancer. The PTEN p.W111* mutant allele fractions were lowest in benign, inactive endometrial glands (0.7%), highest in adenocarcinoma (36.9%), and, notably, were always markedly reduced following progesterone treatment. To our knowledge, this report provides the first molecular characterization of EndoCA development in a single patient. A single PTEN mutation was present throughout the 12 years of cancer development. Importantly, and with potential significance toward medical and nonsurgical management of EndoCA, progesterone treatments were consistently noted to markedly decrease PTEN mutant allele fractions to precancerous levels.

求助全文
通过发布文献求助,成功后即可免费获取论文全文。 去求助
来源期刊
Cold Spring Harbor Molecular Case Studies
Cold Spring Harbor Molecular Case Studies MEDICINE, RESEARCH & EXPERIMENTAL-
CiteScore
3.20
自引率
0.00%
发文量
54
期刊介绍: Cold Spring Harbor Molecular Case Studies is an open-access, peer-reviewed, international journal in the field of precision medicine. Articles in the journal present genomic and molecular analyses of individuals or cohorts alongside their clinical presentations and phenotypic information. The journal''s purpose is to rapidly share insights into disease development and treatment gained by application of genomics, proteomics, metabolomics, biomarker analysis, and other approaches. The journal covers the fields of cancer, complex diseases, monogenic disorders, neurological conditions, orphan diseases, infectious disease, gene therapy, and pharmacogenomics. It has a rapid peer-review process that is based on technical evaluation of the analyses performed, not the novelty of findings, and offers a swift, clear path to publication. The journal publishes: Research Reports presenting detailed case studies of individuals and small cohorts, Research Articles describing more extensive work using larger cohorts and/or functional analyses, Rapid Communications presenting the discovery of a novel variant and/or novel phenotype associated with a known disease gene, Rapid Cancer Communications presenting the discovery of a novel variant or combination of variants in a cancer type, Variant Discrepancy Resolution describing efforts to resolve differences or update variant interpretations in ClinVar through case-level data sharing, Follow-up Reports linked to previous observations, Plus Review Articles, Editorials, and Position Statements on best practices for research in precision medicine.
期刊最新文献
Rapid genome diagnosis of alveolar capillary dysplasia leading to treatment in a child with respiratory and cardiac failure. Reclassification of the HPGD p.Ala13Glu variant causing primary hypertrophic osteoarthropathy. The importance of escalating molecular diagnostics in patients with low-grade pediatric brain cancer. Novel pathogenic PDX1 gene variant in a Korean family with maturity-onset diabetes of the young. Novel pathogenic UQCRC2 variants in a female with normal neurodevelopment.
×
引用
GB/T 7714-2015
复制
MLA
复制
APA
复制
导出至
BibTeX EndNote RefMan NoteFirst NoteExpress
×
×
提示
您的信息不完整,为了账户安全,请先补充。
现在去补充
×
提示
您因"违规操作"
具体请查看互助需知
我知道了
×
提示
现在去查看 取消
×
提示
确定
0
微信
客服QQ
Book学术公众号 扫码关注我们
反馈
×
意见反馈
请填写您的意见或建议
请填写您的手机或邮箱
已复制链接
已复制链接
快去分享给好友吧!
我知道了
×
扫码分享
扫码分享
Book学术官方微信
Book学术文献互助
Book学术文献互助群
群 号:481959085
Book学术
文献互助 智能选刊 最新文献 互助须知 联系我们:info@booksci.cn
Book学术提供免费学术资源搜索服务,方便国内外学者检索中英文文献。致力于提供最便捷和优质的服务体验。
Copyright © 2023 Book学术 All rights reserved.
ghs 京公网安备 11010802042870号 京ICP备2023020795号-1