镰状细胞病:从遗传学到治疗方法。

IF 7.7 2区 生物学 Q1 GENETICS & HEREDITY Annual review of genomics and human genetics Pub Date : 2023-08-25 DOI:10.1146/annurev-genom-120122-081037
Giulia Hardouin, Elisa Magrin, Alice Corsia, Marina Cavazzana, Annarita Miccio, Michaela Semeraro
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引用次数: 0

摘要

镰状细胞病(SCD)是一种由β-珠蛋白编码基因点突变引起的单基因血液病。异常血红蛋白[镰状血红蛋白(HbS)]在低氧条件下聚合并导致红细胞呈镰状。临床表现从非常严重(伴有急性疼痛、慢性疼痛和早期死亡)到正常(很少并发症和正常寿命)不等。SCD的变异性可能(部分)归因于各种遗传调节剂。首先,我们回顾了影响珠蛋白表达或以其他方式调节SCD严重程度的主要遗传因素、多态性和修饰基因。考虑到SCD是一种复杂的,多因素的疾病,对于开发适当的药物和基因治疗是重要的。其次,我们回顾了SCD基因治疗最新进展的特点、优缺点,从基于慢病毒载体的方法到基因编辑策略。
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Sickle Cell Disease: From Genetics to Curative Approaches.

Sickle cell disease (SCD) is a monogenic blood disease caused by a point mutation in the gene coding for β-globin. The abnormal hemoglobin [sickle hemoglobin (HbS)] polymerizes under low-oxygen conditions and causes red blood cells to sickle. The clinical presentation varies from very severe (with acute pain, chronic pain, and early mortality) to normal (few complications and a normal life span). The variability of SCD might be due (in part) to various genetic modulators. First, we review the main genetic factors, polymorphisms, and modifier genes that influence the expression of globin or otherwise modulate the severity of SCD. Considering SCD as a complex, multifactorial disorder is important for the development of appropriate pharmacological and genetic treatments. Second, we review the characteristics, advantages, and disadvantages of the latest advances in gene therapy for SCD, from lentiviral-vector-based approaches to gene-editing strategies.

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来源期刊
CiteScore
14.90
自引率
1.10%
发文量
29
期刊介绍: Since its inception in 2000, the Annual Review of Genomics and Human Genetics has been dedicated to showcasing significant developments in genomics as they pertain to human genetics and the human genome. The journal emphasizes genomic technology, genome structure and function, genetic modification, human variation and population genetics, human evolution, and various aspects of human genetic diseases, including individualized medicine.
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