克莱夫斯特拉综合征患者无功能退化的精神病和自闭症。

IF 1.5 4区 医学 Q4 GENETICS & HEREDITY Psychiatric Genetics Pub Date : 2023-02-01 DOI:10.1097/YPG.0000000000000330
Mark A Colijn, Cherelyn M Lakusta, Julien L Marcadier
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引用次数: 1

摘要

Kleefstra综合征是一种罕见的遗传性疾病,由常染色质组蛋白赖氨酸甲基转移酶1 (EHMT1)基因单倍不足引起。它的特点是各种畸形特征,共病的医疗问题和发育迟缓/智力残疾。神经精神症状也可能出现,包括自闭症特征和精神病,并常伴有功能退化。然而,这种综合征的精神症状的现象学尚未在文献中得到很好的描述。因此,在这篇简短的报告中,我们回顾了有关Kleefstra综合征中精神病发生的文献,并描述了一位35岁患有智力残疾、自闭症谱系障碍和精神分裂症(与躁狂特征相关)的男性患者的症状概况。这是第一个报告精神病症状完全缓解响应zuclopenthixol治疗个体Kleefstra综合征。这个病例也很独特,因为它表明,在受影响的个体中,功能退化并不一定与精神分裂症样表现的发展相一致。
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Psychosis and autism without functional regression in a patient with Kleefstra syndrome.

Kleefstra syndrome is a rare genetic disorder caused by haploinsufficiency of the euchromatic histone lysine methyltransferase 1 (EHMT1) gene. It is characterized by a variety of dysmorphic features, comorbid medical issues, and developmental delays/intellectual disability. Neuropsychiatric symptoms may also occur, including autistic features and psychosis, and are often accompanied by functional regression. However, the phenomenology of psychotic symptoms in this syndrome has not been well described in the literature. As such, in this brief report, we review the literature with respect to the occurrence of psychosis in Kleefstra syndrome and describe the symptom profile of a 35-year-old affected male with an intellectual disability, autism spectrum disorder, and schizophrenia (in association with manic features). This is the first report of psychotic symptoms fully remitting in response to zuclopenthixol therapy in an individual with Kleefstra syndrome. This case is also unique as it demonstrates that functional regression does not necessarily coincide with the development of schizophrenia-like presentations in affected individuals.

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来源期刊
Psychiatric Genetics
Psychiatric Genetics 医学-神经科学
CiteScore
2.30
自引率
0.00%
发文量
39
审稿时长
3 months
期刊介绍: ​​​​​​The journal aims to publish papers which bring together clinical observations, psychological and behavioural abnormalities and genetic data. All papers are fully refereed. Psychiatric Genetics is also a forum for reporting new approaches to genetic research in psychiatry and neurology utilizing novel techniques or methodologies. Psychiatric Genetics publishes original Research Reports dealing with inherited factors involved in psychiatric and neurological disorders. This encompasses gene localization and chromosome markers, changes in neuronal gene expression related to psychiatric disease, linkage genetics analyses, family, twin and adoption studies, and genetically based animal models of neuropsychiatric disease. The journal covers areas such as molecular neurobiology and molecular genetics relevant to mental illness. Reviews of the literature and Commentaries in areas of current interest will be considered for publication. Reviews and Commentaries in areas outside psychiatric genetics, but of interest and importance to Psychiatric Genetics, will also be considered. Psychiatric Genetics also publishes Book Reviews, Brief Reports and Conference Reports.
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