{"title":"肺泡蛋白病和新的治疗理念。","authors":"Claudio Rodriguez Gonzalez, Hannah Schevel, Gesine Hansen, Nicolaus Schwerk, Nico Lachmann","doi":"10.1055/a-2233-1243","DOIUrl":null,"url":null,"abstract":"<p><p>Pulmonary alveolar proteinosis (PAP) is an umbrella term used to refer to a pulmonary syndrome which is characterized by excessive accumulation of surfactant in the lungs of affected individuals. In general, PAP is a rare lung disease affecting children and adults, although its prevalence and incidence is variable among different countries. Even though PAP is a rare disease, it is a prime example on how modern medicine can lead to new therapeutic concepts, changing ways and techniques of (genetic) diagnosis which ultimately led into personalized treatments, all dedicated to improve the function of the impaired lung and thus life expectancy and quality of life in PAP patients. In fact, new technologies, such as new sequencing technologies, gene therapy approaches, new kind and sources of stem cells and completely new insights into the ontogeny of immune cells such as macrophages have increased our understanding in the onset and progression of PAP, which have paved the way for novel therapeutic concepts for PAP and beyond. As of today, classical monocyte-derived macrophages are known as important immune mediator and immune sentinels within the innate immunity. Furthermore, macrophages (known as tissue resident macrophages (TRMs)) can also be found in various tissues, introducing e. g. alveolar macrophages in the broncho-alveolar space as crucial cellular determinants in the onset of PAP and other lung disorders. Given recent insights into the onset of alveolar macrophages and knowledge about factors which impede their function, has led to the development of new therapies, which are applied in the context of PAP, with promising implications also for other diseases in which macrophages play an important role. 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引用次数: 0
摘要
肺泡蛋白沉积症(PAP)是一个统称,指一种肺部综合征,其特点是患者肺部表面活性物质过度积聚。一般来说,肺泡蛋白沉积症是一种罕见的肺部疾病,多发于儿童和成人,但其流行率和发病率因国家而异。尽管 PAP 是一种罕见疾病,但它却是现代医学如何引领新的治疗理念、改变(基因)诊断方法和技术并最终实现个性化治疗的典型例子,所有这些都致力于改善受损肺部的功能,从而提高 PAP 患者的预期寿命和生活质量。事实上,新的技术,如新的测序技术、基因治疗方法、新的干细胞种类和来源,以及对免疫细胞(如巨噬细胞)本体的全新认识,提高了我们对 PAP 发病和进展的了解,为 PAP 及其他疾病的新型治疗理念铺平了道路。众所周知,源自单核细胞的经典巨噬细胞是先天性免疫中重要的免疫介质和免疫哨兵。此外,巨噬细胞(被称为组织常驻巨噬细胞(TRMs))也存在于各种组织中,例如,支气管肺泡空间中的肺泡巨噬细胞是 PAP 和其他肺部疾病发病的关键细胞决定因素。鉴于最近对肺泡巨噬细胞发病的深入了解以及对阻碍其功能的因素的认识,人们开发出了新的疗法,这些疗法被用于治疗 PAP,并对巨噬细胞在其中发挥重要作用的其他疾病产生了积极的影响。因此,我们在此总结了对各种形式的肺结核的最新认识,并介绍了目前在肺结核框架内开展的新的临床前研究工作,从而为仍然罹患这种严重的、可能危及生命的疾病的儿童和成人介绍新的疗法。
Pulmonary Alveolar Proteinosis and new therapeutic concepts.
Pulmonary alveolar proteinosis (PAP) is an umbrella term used to refer to a pulmonary syndrome which is characterized by excessive accumulation of surfactant in the lungs of affected individuals. In general, PAP is a rare lung disease affecting children and adults, although its prevalence and incidence is variable among different countries. Even though PAP is a rare disease, it is a prime example on how modern medicine can lead to new therapeutic concepts, changing ways and techniques of (genetic) diagnosis which ultimately led into personalized treatments, all dedicated to improve the function of the impaired lung and thus life expectancy and quality of life in PAP patients. In fact, new technologies, such as new sequencing technologies, gene therapy approaches, new kind and sources of stem cells and completely new insights into the ontogeny of immune cells such as macrophages have increased our understanding in the onset and progression of PAP, which have paved the way for novel therapeutic concepts for PAP and beyond. As of today, classical monocyte-derived macrophages are known as important immune mediator and immune sentinels within the innate immunity. Furthermore, macrophages (known as tissue resident macrophages (TRMs)) can also be found in various tissues, introducing e. g. alveolar macrophages in the broncho-alveolar space as crucial cellular determinants in the onset of PAP and other lung disorders. Given recent insights into the onset of alveolar macrophages and knowledge about factors which impede their function, has led to the development of new therapies, which are applied in the context of PAP, with promising implications also for other diseases in which macrophages play an important role. Thus, we here summarize the latest insights into the various forms of PAP and introduce new pre-clinical work which is currently conducted in the framework of PAP, introducing new therapies for children and adults who still suffer from this severe, potentially life-threatening disease.
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