Giby V George, Maggie Kajstura, Andrew G Evans, Chauncey R Syposs
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引用次数: 0
摘要
γδ(γδ)T 细胞急性淋巴细胞白血病/淋巴瘤(T-ALL)是 T 淋巴细胞白血病中一种罕见的侵袭性亚型,仅占所有 T-ALL 病例的 9-12%。在此,我们报告了一例 8 岁男孩的病例,他出现面部肿胀、呼吸急促、进行性颈部和腋窝淋巴结病变。病理检查、流式细胞术(Navios、Beckman Coulter ClearLLab 10C 10 色 T 细胞面板[含 FITC 标记的 TCR γδ 抗体])、染色体分析、间期 FISH 和基于 DNA 的靶向 NGS(34 基因 Illumina TruSeq 髓系面板)均已完成。淋巴结活检标本的流式细胞术评估显示,未成熟T细胞群的CD4、CD3、CD2(亚群阳性)、CD5、CD7、CD38、CD1a、细胞质末端脱氧核苷酸转移酶(cyto-TdT)、CD30(亚群阳性)和T细胞受体(TCR)γδ(γδ)阳性。对肿大的淋巴结和骨髓进行的显微镜检查显示,肿瘤呈密集、弥漫性浸润。相间荧光原位杂交(FISH)发现,90.5%的相间核中存在 PDGFRB(5q32)拷贝数缺失。基于DNA的靶向NGS检测出NOTCH1的二级致癌变异(c.7375C > T, p.Gln2459Ter),VAF为21%。这例γδ T-ALL病例突显了一种罕见的实体,并增加了文献(尽管很少),这可能有助于更好地识别和分类。
Gamma-delta T-cell acute lymphoblastic lymphoma/leukemia: a report of a rare entity.
Gamma delta (γδ) T-cell acute lymphoblastic leukemia/lymphoma (T-ALL) is a rare, aggressive subtype of T-lymphoid leukemia that accounts for only 9-12% of all T-ALL cases. Herein, we report the case of an 8-year-old boy who presented with facial swelling, shortness of breath, and progressive cervical and axillary lymphadenopathy. Pathological examination, flow cytometry (Navios, Beckman Coulter ClearLLab 10C 10-color T-cell panel [containing FITC-labeled TCR γδ antibody]), chromosomal analysis, interphase FISH, and targeted DNA-based NGS (34-gene Illumina TruSeq Myeloid Panel) were performed. Flow cytometry evaluation of a lymph node biopsy specimen revealed an immature T-cell population positive for CD4, CD3, CD2 (subset positive), CD5, CD7, CD38, CD1a, cytoplasmic terminal deoxynucleotidyl transferase (cyto-TdT), CD30 (subset positive), and T-cell receptor (TCR) gamma delta (γδ). Microscopic examination of an enlarged lymph node and bone marrow showed involvement by a dense, diffuse, neoplastic infiltrate. Interphase FISH revealed a copy number loss of PDGFRB (5q32) in 90.5% of interphase nuclei. Targeted DNA-based NGS detected a tier II oncogenic variant in NOTCH1 (c.7375C > T, p.Gln2459Ter) at a VAF of 21%. This case of γδ T-ALL highlights a rare entity and adds to the literature, albeit scant, which may aid in better recognition and classification.
期刊介绍:
The Journal of Hematopathology aims at providing pathologists with a special interest in hematopathology with all the information needed to perform modern pathology in evaluating lymphoid tissues and bone marrow. To this end the journal publishes reviews, editorials, comments, original papers, guidelines and protocols, papers on ancillary techniques, and occasional case reports in the fields of the pathology, molecular biology, and clinical features of diseases of the hematopoietic system.
The journal is the unique reference point for all pathologists with an interest in hematopathology. Molecular biologists involved in the expanding field of molecular diagnostics and research on lymphomas and leukemia benefit from the journal, too. Furthermore, the journal is of major interest for hematologists dealing with patients suffering from lymphomas, leukemias, and other diseases.
The journal is unique in its true international character. Especially in the field of hematopathology it is clear that there are huge geographical variations in incidence of diseases. This is not only locally relevant, but due to globalization, relevant for all those involved in the management of patients.