Mohd P Khan, Elena Sabini, Katherine Beigel, Giulia Lanzolla, Brittany Laslow, Dian Wang, Christophe Merceron, Amato Giaccia, Fanxin Long, Deanne Taylor, Ernestina Schipani
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TFAM-deficient mice presented with thinner cortical bone, spontaneous midshaft fractures, and compromised periosteal cell bioenergetics, characterized by reduced ATP levels. Additionally, they exhibited an enlarged periosteal progenitor cell pool with impaired osteoblast differentiation. Increasing hypoxia-inducible factor 1a (HIF1) activity within periosteal cells substantially mitigated the detrimental effects induced by TFAM deletion. HIF1 is known to promote glycolysis in all cell types. Our findings underscore the indispensability of OxPhos for the proper accrual of cortical bone mass and indicate a compensatory mechanism between OxPhos and glycolysis in periosteal cells. 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引用次数: 0
摘要
通过氧化磷酸化(OxPhos)和糖酵解等途径进行的能量代谢在细胞分化和功能中发挥着关键作用。我们的研究通过删除线粒体转录因子 A (TFAM),探讨了 OxPhos 中断对皮质骨发育的影响。TFAM 通过调节线粒体基因的转录来控制 OxPhos。骨皮质是长骨的坚硬外壳,由骨膜包裹,骨膜是一种结缔组织层,其中充满了骨骼祖细胞,这些祖细胞可催生成骨细胞(骨形成细胞)。缺乏 TFAM 的小鼠皮质骨较薄,会出现自发性中轴骨折,骨膜细胞生物能受损,表现为 ATP 水平降低。此外,它们还表现出骨膜祖细胞池扩大,成骨细胞分化受损。提高骨膜细胞中缺氧诱导因子1a(HIF1)的活性可显著减轻TFAM缺失诱导的有害影响。众所周知,HIF1能促进所有类型细胞的糖酵解。我们的研究结果强调了 OxPhos 对皮质骨量的正常累积的不可或缺性,并表明了骨膜细胞中 OxPhos 和糖酵解之间的补偿机制。这项研究为了解能量代谢与骨骼健康之间的关系开辟了新的途径,并表明调节生物能途径可为骨质脆弱的病症提供治疗途径。
HIF1 activation safeguards cortical bone formation against impaired oxidative phosphorylation.
Energy metabolism, through pathways such as oxidative phosphorylation (OxPhos) and glycolysis, plays a pivotal role in cellular differentiation and function. Our study investigates the impact of OxPhos disruption in cortical bone development by deleting mitochondrial transcription factor A (TFAM). TFAM controls OxPhos by regulating the transcription of mitochondrial genes. The cortical bone, constituting the long bones' rigid shell, is sheathed by the periosteum, a connective tissue layer populated with skeletal progenitors that spawn osteoblasts, the bone-forming cells. TFAM-deficient mice presented with thinner cortical bone, spontaneous midshaft fractures, and compromised periosteal cell bioenergetics, characterized by reduced ATP levels. Additionally, they exhibited an enlarged periosteal progenitor cell pool with impaired osteoblast differentiation. Increasing hypoxia-inducible factor 1a (HIF1) activity within periosteal cells substantially mitigated the detrimental effects induced by TFAM deletion. HIF1 is known to promote glycolysis in all cell types. Our findings underscore the indispensability of OxPhos for the proper accrual of cortical bone mass and indicate a compensatory mechanism between OxPhos and glycolysis in periosteal cells. The study opens new avenues for understanding the relationship between energy metabolism and skeletal health and suggests that modulating bioenergetic pathways may provide a therapeutic avenue for conditions characterized by bone fragility.
期刊介绍:
JCI Insight is a Gold Open Access journal with a 2022 Impact Factor of 8.0. It publishes high-quality studies in various biomedical specialties, such as autoimmunity, gastroenterology, immunology, metabolism, nephrology, neuroscience, oncology, pulmonology, and vascular biology. The journal focuses on clinically relevant basic and translational research that contributes to the understanding of disease biology and treatment. JCI Insight is self-published by the American Society for Clinical Investigation (ASCI), a nonprofit honor organization of physician-scientists founded in 1908, and it helps fulfill the ASCI's mission to advance medical science through the publication of clinically relevant research reports.