自闭症多基因评分与成人小脑和脑干体积磁共振成像表型的关联。

IF 6.3 1区 医学 Q1 GENETICS & HEREDITY Molecular Autism Pub Date : 2024-08-07 DOI:10.1186/s13229-024-00611-7
Salahuddin Mohammad, Mélissa Gentreau, Manon Dubol, Gull Rukh, Jessica Mwinyi, Helgi B Schiöth
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引用次数: 0

摘要

以往关于自闭症谱系障碍(ASD)的研究显示,小脑和脑干的体积发生了重要变化。然而,这些研究大多局限于病例对照研究,临床样本较少,且主要包括儿童或青少年。在此,我们的目的是在人群水平上探讨 ASD 的累积遗传负荷(多基因风险评分,PRS)与小脑和脑干的体积变化以及成人大脑的整体脑组织体积之间的关联。我们利用了精神病遗传学联盟最新的 ASD 全基因组关联研究(18381 例病例,27969 例对照),并在英国生物库这一独立队列中构建了 ASD PRS。为了研究约 31,000 名参与者中 ASD PRS 与 44 种脑磁共振成像(MRI)表型之间的关联,我们进行了回归分析,控制多重比较,假发现率 (FDR) 为 5%。主要分析包括十六种 MRI 表型:大脑总体积、脑脊液 (CSF)、灰质 (GM)、白质 (WM)、整个小脑的 GM、脑干以及小脑的十个区域(I_IV、V、VI、VIIb、VIIIa、VIIIb、IX、X、CrusI 和 CrusII)。二次分析包括 28 种磁共振成像表型:小脑的亚区域体积,包括蚓部 GM 和每个小脑区域的左右小叶。ASD PRS与七个脑区的体积明显相关,PRS越高,全脑、WM、脑干、小脑I-IV、IX和X区的体积越小,脑脊液体积越大。包括左侧小脑小叶 I-IV、小脑蚓部 VIIIb 和 X 在内的三个子区域的体积与 ASD PRS 呈显著负相关。该研究强调了 ASD 易感性、其潜在的遗传病因和成人大脑神经解剖结构改变之间的重要联系。
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Association of polygenic scores for autism with volumetric MRI phenotypes in cerebellum and brainstem in adults.

Previous research on autism spectrum disorders (ASD) have showed important volumetric alterations in the cerebellum and brainstem. Most of these studies are however limited to case-control studies with small clinical samples and including mainly children or adolescents. Herein, we aimed to explore the association between the cumulative genetic load (polygenic risk score, PRS) for ASD and volumetric alterations in the cerebellum and brainstem, as well as global brain tissue volumes of the brain among adults at the population level. We utilized the latest genome-wide association study of ASD by the Psychiatric Genetics Consortium (18,381 cases, 27,969 controls) and constructed the ASD PRS in an independent cohort, the UK Biobank. Regression analyses controlled for multiple comparisons with the false-discovery rate (FDR) at 5% were performed to investigate the association between ASD PRS and forty-four brain magnetic resonance imaging (MRI) phenotypes among ~ 31,000 participants. Primary analyses included sixteen MRI phenotypes: total volumes of the brain, cerebrospinal fluid (CSF), grey matter (GM), white matter (WM), GM of whole cerebellum, brainstem, and ten regions of the cerebellum (I_IV, V, VI, VIIb, VIIIa, VIIIb, IX, X, CrusI and CrusII). Secondary analyses included twenty-eight MRI phenotypes: the sub-regional volumes of cerebellum including the GM of the vermis and both left and right lobules of each cerebellar region. ASD PRS were significantly associated with the volumes of seven brain areas, whereby higher PRS were associated to reduced volumes of the whole brain, WM, brainstem, and cerebellar regions I-IV, IX, and X, and an increased volume of the CSF. Three sub-regional volumes including the left cerebellar lobule I-IV, cerebellar vermes VIIIb, and X were significantly and negatively associated with ASD PRS. The study highlights a substantial connection between susceptibility to ASD, its underlying genetic etiology, and neuroanatomical alterations of the adult brain.

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来源期刊
Molecular Autism
Molecular Autism GENETICS & HEREDITY-NEUROSCIENCES
CiteScore
12.10
自引率
1.60%
发文量
44
审稿时长
17 weeks
期刊介绍: Molecular Autism is a peer-reviewed, open access journal that publishes high-quality basic, translational and clinical research that has relevance to the etiology, pathobiology, or treatment of autism and related neurodevelopmental conditions. Research that includes integration across levels is encouraged. Molecular Autism publishes empirical studies, reviews, and brief communications.
期刊最新文献
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