新型亚甲基四氢叶酸还原酶(MTHFR)突变,表现为新生儿脑病、脱发和马凡诺特征。

IF 0.6 Q3 MEDICINE, GENERAL & INTERNAL BMJ Case Reports Pub Date : 2024-10-02 DOI:10.1136/bcr-2024-261755
Vimesh Parmar, Arunkumarendu Singh, Rinkal Madhudiya
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引用次数: 0

摘要

我们接诊了一例患有嗜睡、肌张力低下、通气不足和严重脑病的男性足月新生儿。该婴儿的两个兄弟姐妹在新生儿期死亡,死因不明。婴儿的皮肤和毛发异常,包括四肢脱皮、角化性口炎、颊炎、新生儿痤疮和稀疏的毛发。此外,婴儿身材高大,手指和脚趾细长,面部畸形,脸部狭长,睑间距增大。病情迅速恶化,不幸的是,在确诊之前就已经死亡。串联质谱分析表明该患者蛋氨酸含量低,临床外显子测序发现其MTHFR基因存在无义突变。
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Novel methylenetetrahydrofolate reductase (MTHFR) mutation presenting with neonatal encephalopathy, hair loss and marfanoid features.

We present a case of a male term neonate with lethargy, hypotonia, hypoventilation and severe encephalopathy. The infant had a history of two siblings who died in the neonatal period from unclear causes. The infant exhibited skin and hair abnormalities, including desquamation of the extremities, angular stomatitis, cheilitis, neonatal acne and thin, sparse hair. Additionally, the infant had a tall stature; long, slender fingers and toes; and facial dysmorphism characterised by a long, narrow face with increased interpalpebral distance. The condition deteriorated rapidly, and unfortunately, death occurred before a definitive diagnosis could be established. Tandem mass spectrometry suggested low methionine and clinical exome sequencing identified a nonsense mutation in the MTHFR gene.

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来源期刊
BMJ Case Reports
BMJ Case Reports Medicine-Medicine (all)
CiteScore
1.40
自引率
0.00%
发文量
1588
期刊介绍: BMJ Case Reports is an important educational resource offering a high volume of cases in all disciplines so that healthcare professionals, researchers and others can easily find clinically important information on common and rare conditions. All articles are peer reviewed and copy edited before publication. BMJ Case Reports is not an edition or supplement of the BMJ.
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