小脑共济失调、神经病变和前庭反射症是一种新的DNMT1突变的表现。

IF 2.7 3区 医学 Q3 NEUROSCIENCES Cerebellum Pub Date : 2025-01-04 DOI:10.1007/s12311-024-01780-0
Jake Sossamon, Patrick O'Connell, David P W Rastall
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引用次数: 0

摘要

一位50岁的女性,有20年的步态不稳定史,新发眩晕和示波器。检查显示双侧前庭功能丧失,小脑共济失调,感觉神经病变,“是-是”型头颤,眼球震颤和类似综合征的家族史。小脑性共济失调伴神经病变和双侧前庭反射综合征(RFC1)的基因检测结果为阴性,但全外显子组测序发现DNA甲基转移酶1 (DNMT1)基因的新突变,拓宽了该表型的鉴别诊断。治疗的重点是对症治疗和遗传咨询。该病例强调了在具有相似临床表现的患者中考虑DNMT1突变的重要性。
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Cerebellar Ataxia, Neuropathy, and Vestibular Areflexia as a Presentation of a Novel DNMT1 Mutation.

A 50-year-old woman with a 20-year history of gait instability presented with new-onset vertigo and oscillopsia. Examination revealed bilateral vestibular loss, cerebellar ataxia, sensory neuropathy, a "yes-yes" head tremor, nystagmus and a family history of a similar syndrome. Genetic testing for cerebellar ataxia with neuropathy and bilateral vestibular areflexia syndrome (RFC1) was negative, but whole exome sequencing identified a novel mutation in the DNA methyltransferase 1 (DNMT1) gene, broadening the differential diagnosis for this phenotype. Management was focused on symptomatic treatment and genetic counseling. This case highlights the importance of considering DNMT1 mutations in patients with a similar clinical presentation.

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来源期刊
Cerebellum
Cerebellum 医学-神经科学
CiteScore
6.40
自引率
14.30%
发文量
150
审稿时长
4-8 weeks
期刊介绍: Official publication of the Society for Research on the Cerebellum devoted to genetics of cerebellar ataxias, role of cerebellum in motor control and cognitive function, and amid an ageing population, diseases associated with cerebellar dysfunction. The Cerebellum is a central source for the latest developments in fundamental neurosciences including molecular and cellular biology; behavioural neurosciences and neurochemistry; genetics; fundamental and clinical neurophysiology; neurology and neuropathology; cognition and neuroimaging. The Cerebellum benefits neuroscientists in molecular and cellular biology; neurophysiologists; researchers in neurotransmission; neurologists; radiologists; paediatricians; neuropsychologists; students of neurology and psychiatry and others.
期刊最新文献
Emerging Deep Brain Stimulation Targets in the Cerebellum for Tremor. Assessment of Peripheral Neuropathy Using Current Perception Threshold Measurement in Patients with Spinocerebellar Ataxia Type 3. Tremor in the Age of Omics: An Overview of the Transcriptomic Landscape of Essential Tremor. Spontaneous Nystagmus Violating the Alexander's Law: Neural Substrates and Mechanisms. Causally Mapping the Cerebellum in Children and Young Adults: from Motor to Cognition.
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