抗中性粒细胞胞浆抗体相关性血管炎的肿块形成变异:肉芽肿病的诊断难题。病例报告。

IF 2.9 Q2 RHEUMATOLOGY ACR open rheumatology Pub Date : 2025-04-01 DOI:10.1002/acr2.70038
Benedetta Fazzi, Elena Treppo, Simone Longhino, Maria Pillon, Luca Quartuccio
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引用次数: 0

摘要

2018年,一名中年妇女因乳房肉芽肿病变就诊。到2021年,抗生素耐药性肺炎导致肺部和甲状腺的肉芽肿性炎症被发现。最初误诊为埃尔德海姆-切斯特病(ECD),她接受了干扰素治疗,但没有成功。组织病理学后来排除了ECD,提示一种未明确的肉芽肿性疾病,肉芽肿病合并多血管炎(GPA)最初因抗中性粒细胞胞浆抗体(ANCAs)阴性和泡沫组织细胞而被排除。2023年,重复肺活检和PR3-ANCA阳性导致修订诊断为团块形成的GPA。利妥昔单抗治疗导致缓解。本病例突出了GPA诊断的复杂性,具有不典型的组织病理学特征。
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Mass-Forming Variants in Antineutrophil Cytoplasmic Antibody-Associated Vasculitis: Diagnostic Complexities in Granulomatous Disease. A Case Report.

A middle-aged woman presented with a granulomatous breast lesion in 2018. By 2021, antibiotic-resistant pneumonia led to the discovery of granulomatous inflammation in the lung and thyroid. Initially misdiagnosed as Erdheim-Chester disease (ECD), she was treated with interferon without success. Histopathology later ruled out ECD, suggesting an unspecified granulomatous disease, with granulomatosis with polyangiitis (GPA) initially excluded due to negative antineutrophil cytoplasmic antibodies (ANCAs) and foamy histiocytes. In 2023, repeated lung biopsy and PR3-ANCA positivity led to a revised diagnosis of mass-forming GPA. Rituximab therapy resulted in remission. This case highlights the diagnostic complexity of GPA with atypical histopathological features.

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CiteScore
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