甘氨酸受体抗体与乳糜泻相关的神经功能障碍。

Q3 Medicine Cerebellum and Ataxias Pub Date : 2021-05-03 DOI:10.1186/s40673-021-00135-3
Lewis Kass-Iliyya, Ptolemaios G Sarrigiannis, David S Sanders, Marios Hadjivassiliou
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引用次数: 0

摘要

麸质敏感性可表现为一系列神经功能障碍,包括共济失调、脑病和伴有或不伴有乳糜泻(CD)的神经病变。谷蛋白敏感性也可表现为中枢神经系统(CNS)的高兴奋性和皮质肌阵挛,这通常伴有难愈性乳糜泻。中枢神经系统的高兴奋性也可与谷氨酸脱羧酶(GAD)抗体或较少与甘氨酸受体抗体(GlyR-Abs)有关,但这些抗体的直接致病作用仍有争议。我们之前报道过麸质敏感性和抗广泛性焦虑症相关共济失调之间的联系,这种联系随着无麸质饮食的采用而改善。目前尚不清楚麸质驱动的中枢神经系统过度兴奋性与GlyR-Abs的存在之间是否存在类似的联系。我们报告两例CD表现为中枢神经系统高兴奋性和相关的GlyR-Abs。除了共济失调和皮质肌阵挛外,还有1例难治性CD患者死于肠病相关t细胞淋巴瘤。另一位患者通过严格的无麸质饮食不仅改善了病情,而且血清学上显示循环GlyR-Abs的消除。我们得出结论,谷蛋白敏感性和glyr - abs相关的中枢神经系统高兴奋性之间存在相互作用,对于此类患者,无谷蛋白饮食是一种重要的治疗干预。通过采用无麸质饮食消除GlyR-Abs表明这些抗体可能是一种附带现象,而不是直接涉及发病机制。
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Glycine receptor antibodies and coeliac disease-related neurological dysfunction.

Gluten sensitivity can manifest with a spectrum of neurological dysfunction including ataxia, encephalopathy and neuropathy with or without associated coeliac disease (CD). Gluten sensitivity can also present with central nervous system (CNS) hyperexcitability and cortical myoclonus which is often accompanied with refractory CD. CNS hyperexcitability can also be associated with Glutamic Acid Decarboxylase (GAD) antibodies or much less commonly with Glycine Receptor Antibodies (GlyR-Abs) but the direct pathogenic roles of these antibodies remain debatable. We have previously reported a link between gluten sensitivity and anti-GAD associated ataxia which improves with the adoption of gluten-free diet. It is unclear if a similar link exists between gluten driven CNS hyperexcitability and the presence of GlyR-Abs. We report two cases of CD presenting with CNS hyperexcitability and associated GlyR-Abs. Apart from ataxia and cortical myoclonus, one patient had refractory CD and died from enteropathy-associated T-cell lymphoma. The other patient not only improved with strict gluten-free diet but also showed serological elimination of circulating GlyR-Abs. We conclude that there is an interaction between gluten sensitivity and GlyR-Abs-associated CNS hyperexcitability and in such patients gluten-free diet is an important therapeutic intervention. The elimination of GlyR-Abs by the adoption of gluten free diet suggests that these antibodies may represent an epiphenomenon rather than being directly implicated in the pathogenesis.

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Cerebellum and Ataxias
Cerebellum and Ataxias Medicine-Neurology (clinical)
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