2例非洲土著儿童COL4A5基因突变Alport综合征报告。

IF 0.7 Q4 UROLOGY & NEPHROLOGY Case Reports in Nephrology and Dialysis Pub Date : 2021-10-11 eCollection Date: 2021-09-01 DOI:10.1159/000519076
Emmanuel Oduware, Nosakhare Joyce Iduoriyekemwen, Michael Ibadin, Henry Aikhionbare
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引用次数: 0

摘要

Alport综合征是一种异质性遗传性疾病,累及肾小球基底膜、内耳、视网膜和晶状体囊。典型表现为进行性肾小球病变,常导致终末期肾病、高音调感音神经性耳聋、眼球前晶状体异常、视网膜黄斑出现黄白色斑点和斑点。在本报告中,我们描述了两个兄弟姐妹的病例:15岁和13岁的纯非洲裔男孩,携带COL4A5基因突变。两例患儿均有Alport综合征的典型特征:血尿、蛋白尿、进行性感音神经性高音调听力丧失和眼部异常。他们的肾脏异常最初在血管紧张素转换酶抑制剂治疗后消退,但再次出现,这表明需要早期诊断,因为在提倡严重肾小球病变之前早期采用这种治疗。
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A Case Report of COL4A5 Gene Mutation Alport Syndrome in 2 Native African Children.

Alport syndrome is a heterogeneous genetic disease involving the basement membrane of the glomeruli, inner ear, retina, and lens capsule. It typically manifests as progressive glomerulopathy that frequently results in end-stage renal disease, high-tone sensorineural deafness, and ocular abnormalities of anterior lenticonus and yellow and white dots and flecks on the macular of the retina. In this report, we describe the cases of 2 siblings: 15- and 13-year-old boys of pure African descent with the COL4A5 gene mutation. Both children had the classical features of Alport syndrome haematuria, proteinuria, progressive sensorineural high-tone hearing loss, and ocular abnormalities. Their renal abnormalities initially regressed on therapy with angiotensin-converting enzyme inhibitors but reoccurred, depicting the need for early diagnosis as the early institution of this therapy before significant glomerulopathy is advocated.

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来源期刊
CiteScore
1.20
自引率
0.00%
发文量
36
审稿时长
10 weeks
期刊介绍: This peer-reviewed online-only journal publishes original case reports covering the entire spectrum of nephrology and dialysis, including genetic susceptibility, clinical presentation, diagnosis, treatment or prevention, toxicities of therapy, critical care, supportive care, quality-of-life and survival issues. The journal will also accept case reports dealing with the use of novel technologies, both in the arena of diagnosis and treatment. Supplementary material is welcomed.
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