原发性甲状腺黏液表皮样癌(MEC)在临床、预后和分子上不同于硬化性MEC伴嗜酸性粒细胞增多:一项多中心综合研究

IF 11.3 2区 医学 Q1 ENDOCRINOLOGY & METABOLISM Endocrine Pathology Pub Date : 2023-03-01 DOI:10.1007/s12022-022-09741-1
Hieu Trong Le, Truong P X Nguyen, Mitsuyoshi Hirokawa, Ryohei Katoh, Norisato Mitsutake, Michiko Matsuse, Ayaka Sako, Tetsuo Kondo, Nilesh Vasan, Young Mi Kim, Ying Liu, Lewis Hassell, Kennichi Kakudo, Huy Gia Vuong
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引用次数: 4

摘要

黏液表皮样癌(MEC)和硬化性MEC伴嗜酸性粒细胞增多症(SMECE)是罕见的原发性甲状腺癌。在本研究中,我们旨在展示我们的多中心MEC和SMECE系列,并将我们的数据与已发表的文献相结合,以进一步研究这些肿瘤的临床病理特征和预后。我们在我们的多中心档案中发现了2个mec和4个SMECEs。我们进行了荧光原位杂交(FISH)来确定MAML2基因重排。我们使用Sanger测序和数字聚合酶链反应筛选BRAF、TERT启动子和RAS突变的突变。组织病理学上,mec和SMECEs主要由表皮样细胞和粘液分泌细胞两种类型组成,排列成索状、巢状和小管状。SMECEs的特点是间质致密硬化,含有丰富的嗜酸性粒细胞。我们在所有病例中均未发现任何MAML2融合。2例MEC患者伴有BRAF p.V600E和TERT C228T突变。所有病例均无RAS突变。同时发生另一种甲状腺恶性病灶在mec中更为常见(p
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Primary Thyroid Mucoepidermoid Carcinoma (MEC) Is Clinically, Prognostically, and Molecularly Different from Sclerosing MEC with Eosinophilia: A Multicenter and Integrated Study.

Mucoepidermoid carcinoma (MEC) and sclerosing MEC with eosinophilia (SMECE) are rare primary thyroid carcinomas. In this study, we aimed to present our multicenter series of MEC and SMECE and integrated our data with published literature to further investigate the clinicopathological characteristics and prognoses of these tumors. We found 2 MECs and 4 SMECEs in our multicenter archives. We performed fluorescence in situ hybridization (FISH) to determine the MAML2 gene rearrangement. We screened for mutations in BRAF, TERT promoter, and RAS mutations using Sanger sequencing and digital polymerase chain reaction. Histopathologically, MECs and SMECEs were composed of two main cell types including epidermoid and mucin-secreting cells, arranged in cords, nests, and tubules. SMECEs were characterized by a densely sclerotic stroma with abundant eosinophils. We did not detect any MAML2 fusion in any of our cases. Two MEC cases harbored concomitant BRAF p.V600E and TERT C228T mutations. RAS mutations were absent in all cases. Concurrent foci of another thyroid malignancy were more commonly seen in MECs (p < 0.001), whereas SMECEs were associated with chronic lymphocytic thyroiditis (p < 0.001). MECs and SMECEs had equivalent recurrence-free survival (RFS) but MECs conferred significantly dismal disease-specific survival (DSS) as compared to SMECEs (p = 0.007). In conclusion, MECs and SMECEs not only shared some similarities but also demonstrated differences in clinicopathological characteristics, prognoses, and molecular profiles. SMECEs had a superior DSS in comparison to MECs, suggesting that they are low-grade cancers. This could help clinicians better evaluate patient outcomes and decide appropriate treatment plans.

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来源期刊
Endocrine Pathology
Endocrine Pathology 医学-病理学
CiteScore
12.30
自引率
20.50%
发文量
41
审稿时长
>12 weeks
期刊介绍: Endocrine Pathology publishes original articles on clinical and basic aspects of endocrine disorders. Work with animals or in vitro techniques is acceptable if it is relevant to human normal or abnormal endocrinology. Manuscripts will be considered for publication in the form of original articles, case reports, clinical case presentations, reviews, and descriptions of techniques. Submission of a paper implies that it reports unpublished work, except in abstract form, and is not being submitted simultaneously to another publication. Accepted manuscripts become the sole property of Endocrine Pathology and may not be published elsewhere without written consent from the publisher. All articles are subject to review by experienced referees. The Editors and Editorial Board judge manuscripts suitable for publication, and decisions by the Editors are final.
期刊最新文献
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