Khalilah Mastura Zahari, Nurul 'Ain Masnon, Othmaliza Othman, Kartikasalwah Abd Latif, Noraini Mohd Dusa
{"title":"蝶窦毛细血管瘤伴鞍区和鞍旁延伸的乳头水肿伴急性深度视力丧失——三种罕见的表现","authors":"Khalilah Mastura Zahari, Nurul 'Ain Masnon, Othmaliza Othman, Kartikasalwah Abd Latif, Noraini Mohd Dusa","doi":"10.54029/2023hxu","DOIUrl":null,"url":null,"abstract":"Intracranial capillary haemangioma (ICH) is rare. We report a unique case of a young man with ICH who was presented with papilledema and acute profound visual loss. A 27-year-old man presented with bilateral eye reduced vision for 2 weeks with headaches. Examination showed optic disc swelling with severe visual loss. Neuroimaging revealed a vascular tumour epicentre at the sphenoid sinus with sellar and parasellar extensions. The patient developed massive bleeding during transsphenoidal surgery, in which intraarterial embolization was done, followed by a second surgery. Histopathology revealed benign capillary haemangioma. There was minimal visual improvement. He then developed tumour recurrence at 4 months postoperatively. ICH may cause rapid and acute blindness. Management is challenging with a guarded visual prognosis.","PeriodicalId":49757,"journal":{"name":"Neurology Asia","volume":"72 1","pages":"0"},"PeriodicalIF":0.2000,"publicationDate":"2023-09-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":"0","resultStr":"{\"title\":\"Papilledema with acute profound visual loss in capillary haemangioma of the sphenoid sinus with sellar and parasellar extensions – a triple rarity presentation\",\"authors\":\"Khalilah Mastura Zahari, Nurul 'Ain Masnon, Othmaliza Othman, Kartikasalwah Abd Latif, Noraini Mohd Dusa\",\"doi\":\"10.54029/2023hxu\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"Intracranial capillary haemangioma (ICH) is rare. We report a unique case of a young man with ICH who was presented with papilledema and acute profound visual loss. A 27-year-old man presented with bilateral eye reduced vision for 2 weeks with headaches. Examination showed optic disc swelling with severe visual loss. Neuroimaging revealed a vascular tumour epicentre at the sphenoid sinus with sellar and parasellar extensions. The patient developed massive bleeding during transsphenoidal surgery, in which intraarterial embolization was done, followed by a second surgery. Histopathology revealed benign capillary haemangioma. There was minimal visual improvement. He then developed tumour recurrence at 4 months postoperatively. ICH may cause rapid and acute blindness. Management is challenging with a guarded visual prognosis.\",\"PeriodicalId\":49757,\"journal\":{\"name\":\"Neurology Asia\",\"volume\":\"72 1\",\"pages\":\"0\"},\"PeriodicalIF\":0.2000,\"publicationDate\":\"2023-09-01\",\"publicationTypes\":\"Journal Article\",\"fieldsOfStudy\":null,\"isOpenAccess\":false,\"openAccessPdf\":\"\",\"citationCount\":\"0\",\"resultStr\":null,\"platform\":\"Semanticscholar\",\"paperid\":null,\"PeriodicalName\":\"Neurology Asia\",\"FirstCategoryId\":\"1085\",\"ListUrlMain\":\"https://doi.org/10.54029/2023hxu\",\"RegionNum\":4,\"RegionCategory\":\"医学\",\"ArticlePicture\":[],\"TitleCN\":null,\"AbstractTextCN\":null,\"PMCID\":null,\"EPubDate\":\"\",\"PubModel\":\"\",\"JCR\":\"Q4\",\"JCRName\":\"CLINICAL NEUROLOGY\",\"Score\":null,\"Total\":0}","platform":"Semanticscholar","paperid":null,"PeriodicalName":"Neurology Asia","FirstCategoryId":"1085","ListUrlMain":"https://doi.org/10.54029/2023hxu","RegionNum":4,"RegionCategory":"医学","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":null,"EPubDate":"","PubModel":"","JCR":"Q4","JCRName":"CLINICAL NEUROLOGY","Score":null,"Total":0}
Papilledema with acute profound visual loss in capillary haemangioma of the sphenoid sinus with sellar and parasellar extensions – a triple rarity presentation
Intracranial capillary haemangioma (ICH) is rare. We report a unique case of a young man with ICH who was presented with papilledema and acute profound visual loss. A 27-year-old man presented with bilateral eye reduced vision for 2 weeks with headaches. Examination showed optic disc swelling with severe visual loss. Neuroimaging revealed a vascular tumour epicentre at the sphenoid sinus with sellar and parasellar extensions. The patient developed massive bleeding during transsphenoidal surgery, in which intraarterial embolization was done, followed by a second surgery. Histopathology revealed benign capillary haemangioma. There was minimal visual improvement. He then developed tumour recurrence at 4 months postoperatively. ICH may cause rapid and acute blindness. Management is challenging with a guarded visual prognosis.
期刊介绍:
Neurology Asia (ISSN 1823-6138), previously known as Neurological Journal of South East Asia (ISSN 1394-780X), is the official journal of the ASEAN Neurological Association (ASNA), Asian & Oceanian Association of Neurology (AOAN), and the Asian & Oceanian Child Neurology Association. The primary purpose is to publish the results of study and research in neurology, with emphasis to neurological diseases occurring primarily in Asia, aspects of the diseases peculiar to Asia, and practices of neurology in Asia (Asian neurology).