主动脉瘤和主动脉夹层家族史患者的新型 TGFβR2 剪接变体:病例报告。

Cecilia Vecoli, I. Foffa, Simona Vittorini, N. Botto, Augusto Esposito, Sabrina Costa, Valeria Piagneri, P. Festa, L. Ait-Ali
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引用次数: 0

摘要

我们报告了一名患有主动脉根部和升主动脉扩张、主动脉夹层和猝死阳性家族史的 31 岁男性的临床表现和基因筛查。通过有针对性的多基因面板分析,发现了 TGFβR2 基因剪接受体位点(c.1600-1G>T)上的一个新型杂合变异。生物信息学工具预测,c.1600-1G>T 变体通过改变 - 1 位的剪接受体位点影响前 mRNA 的剪接而致病。这些数据证实了 TGF-β 通路基因的剪接分歧可能是动脉瘤疾病的一个重要过程,并强调了基因测序在识别高危患者方面的实用性,以便对更多的患者进行管理,从而改善遗传性胸主动脉瘤和夹层患者的治疗效果并最大限度地降低成本。
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A novel TGFβR2 splice variant in patient with aortic aneurysm and family history for aortic dissection: a case report.
We report the clinical presentation and genetic screening of a 31-year-old man with dilatation of the aortic root and ascending aorta and a positive family history for aortic dissection and sudden death. A novel heterozygous variant in a splice acceptor site (c.1600-1G>T) of TGFβR2 gene was identified by using a targeted multi-gene panel analysis. Bioinformatics tools predicted that the c.1600-1G>T variant is pathogenic by altering acceptor splice site at - 1 position affecting pre-mRNA splicing. These data confirm that the diverging splicing in the TGF-β pathway genes may be an important process in aneurismal disease and emphasize the utility of genetic sequencing in the identification of high-risk patients for a more patient's management able to improve outcomes and minimize costs for the care of patients with heritable thoracic aortic aneurysm and dissection.
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