PI 5-磷酸酶 SHIP2 基因表达和蛋白溶解度的改变与阿尔茨海默病的病理进展相关。

IF 9.3 1区 医学 Q1 CLINICAL NEUROLOGY Acta Neuropathologica Pub Date : 2024-06-04 DOI:10.1007/s00401-024-02745-7
Kunie Ando, Fahri Küçükali, Emilie Doeraene, Siranjeevi Nagaraj, Eugenia Maria Antonelli, May Thazin Htut, Zehra Yilmaz, Andreea-Claudia Kosa, Lidia Lopez-Guitierrez, Carolina Quintanilla-Sánchez, Emmanuel Aydin, Ana Raquel Ramos, Salwa Mansour, Sabrina Turbant, Stéphane Schurmans, Kristel Sleegers, Christophe Erneux, Jean-Pierre Brion, Karelle Leroy
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引用次数: 0

摘要

最近的一项大型全基因组关联研究发现,表皮生长因子受体(EGFR)(编码表皮生长因子 EGFR)是晚发性注意力缺失症的一个新的遗传风险因素。由 INPPL1 编码的 SHIP2 参与了多种生长因子受体(如表皮生长因子受体)的信号传递和相互作用。虽然 INPPL1 已被确定为 RNA 表达与认知能力下降相关的最重要基因之一,但 SHIP2 的表达和定位在 AD 进展过程中的潜在变化在很大程度上仍不为人所知。在这里,我们报告了表皮生长因子受体和 INPPL1 在 AD 大脑中的基因表达上调。在人类 AD 和 5xFAD 转基因小鼠 AD 模型中,SHIP2 的免疫反应主要在斑块相关的星形胶质细胞和萎缩性神经元中检测到,其增加与淀粉样蛋白负荷相关。虽然INPPL1的mRNA在AD中增加,但SHIP2蛋白的溶解度发生了显著变化,从AD脑匀浆的可溶部分中消失,并与表皮生长因子受体共同富集在不溶部分中。利用基于FRET的流式细胞仪生物传感器检测tau-tau相互作用,SHIP2的过表达显著增加了FRET信号,而siRNA介导的SHIP2的下表达则显著降低了FRET信号。遗传关联分析表明,INPPL1位点的一些变异与CSF pTau水平有关。我们的数据支持这一假设:SHIP2 是表皮生长因子受体和 AD 病理学的中间关键角色,它将人类 AD 中的淀粉样蛋白和 tau 病理学联系在一起。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

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Alteration of gene expression and protein solubility of the PI 5-phosphatase SHIP2 are correlated with Alzheimer's disease pathology progression.

A recent large genome-wide association study has identified EGFR (encoding the epidermal growth factor EGFR) as a new genetic risk factor for late-onset AD. SHIP2, encoded by INPPL1, is taking part in the signalling and interactome of several growth factor receptors, such as the EGFR. While INPPL1 has been identified as one of the most significant genes whose RNA expression correlates with cognitive decline, the potential alteration of SHIP2 expression and localization during the progression of AD remains largely unknown. Here we report that gene expression of both EGFR and INPPL1 was upregulated in AD brains. SHIP2 immunoreactivity was predominantly detected in plaque-associated astrocytes and dystrophic neurites and its increase was correlated with amyloid load in the brain of human AD and of 5xFAD transgenic mouse model of AD. While mRNA of INPPL1 was increased in AD, SHIP2 protein undergoes a significant solubility change being depleted from the soluble fraction of AD brain homogenates and co-enriched with EGFR in the insoluble fraction. Using FRET-based flow cytometry biosensor assay for tau-tau interaction, overexpression of SHIP2 significantly increased the FRET signal while siRNA-mediated downexpression of SHIP2 significantly decreased FRET signal. Genetic association analyses suggest that some variants in INPPL1 locus are associated with the level of CSF pTau. Our data support the hypothesis that SHIP2 is an intermediate key player of EGFR and AD pathology linking amyloid and tau pathologies in human AD.

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来源期刊
Acta Neuropathologica
Acta Neuropathologica 医学-病理学
CiteScore
23.70
自引率
3.90%
发文量
118
审稿时长
4-8 weeks
期刊介绍: Acta Neuropathologica publishes top-quality papers on the pathology of neurological diseases and experimental studies on molecular and cellular mechanisms using in vitro and in vivo models, ideally validated by analysis of human tissues. The journal accepts Original Papers, Review Articles, Case Reports, and Scientific Correspondence (Letters). Manuscripts must adhere to ethical standards, including review by appropriate ethics committees for human studies and compliance with principles of laboratory animal care for animal experiments. Failure to comply may result in rejection of the manuscript, and authors are responsible for ensuring accuracy and adherence to these requirements.
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