Jason Charish, Hidekiyo Harada, Xiaoyan Chen, Thomas Wälchli, Cathy L Barr, Philippe P Monnier
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The Dyslexia-associated gene KIAA0319L is involved in neuronal migration in the developing chick visual system.
The gene KIAA0319-Like (KIAA0319L) is thought to confer susceptibility for developmental dyslexia. Dyslexia may be caused by alterations in neuronal migration, and in utero knockdown of KIAA0319L in rats indicated migration errors. However, studies carried out with KIAA0319L knockout mice did not reveal an altered neuronal migration phenotype. Gene knockout may activate compensatory mechanisms to buffer against genetic mutations during development. Here we assessed the role of KIAA0319L on migrating neurons in the chick developing tectum. Whole mount in situ hybridization was performed for KIAA0319L on embryonic day (E)3 - E5 chick embryos and in situ hybridization on sections was performed at later stages. The specificity and efficiency of engineered microRNA (miRNA) constructs targeting KIAA0319L for knocking down KIAA0319L were verified. miRNAs were electroporated into E5 chick optic tecta. Our studies demonstrate that KIAA0319L is expressed in the developing chick visual system, as well as in the otic vesicles. Knockdown of KIAA0319L in the optic tectum results in abnormal neuronal migration, strengthening the argument that KIAA0319L is involved in this developmental process.
期刊介绍:
The International Journal of Developmental Biology (ISSN: 0214-
6282) is an independent, not for profit scholarly journal, published by
scientists, for scientists. The journal publishes papers which throw
light on our understanding of animal and plant developmental mechanisms in health and disease and, in particular, research which elucidates the developmental principles underlying stem cell properties
and cancer. Technical, historical or theoretical approaches also fall
within the scope of the journal. Criteria for acceptance include scientific excellence, novelty and quality of presentation of data and illustrations. Advantages of publishing in the journal include: rapid
publication; free unlimited color reproduction; no page charges; free
publication of online supplementary material; free publication of audio
files (MP3 type); one-to-one personalized attention at all stages
during the editorial process. An easy online submission facility and an
open online access option, by means of which papers can be published without any access restrictions. In keeping with its mission, the
journal offers free online subscriptions to academic institutions in
developing countries.