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Ectopic Salivary Gland Found in the Vocal Cord: A Rare Case. 声带中发现异位唾液腺:一个罕见病例
IF 0.4 Q4 OTORHINOLARYNGOLOGY Pub Date : 2024-08-14 eCollection Date: 2024-01-01 DOI: 10.1155/2024/4973164
Shori Tajima, Niro Tayama, Fumihiko Matsumoto

Introduction: Ectopic salivary gland is rarely found in the vocal cords; only two cases have been reported in the English literature. To the best of our knowledge, this is the third reported case of this anomaly. Case Presentation. A 78-year-old man with hoarseness two years ago visited our department. There were no other symptoms such as cough or sore throat. He had no history of smoking. Laryngeal endoscopic examination revealed a smooth mass in the anterior right vocal cord. We performed surgery under general anesthesia to remove the polyps and improve hoarseness. The histopathological specimen was reported to be salivary gland tissue. We diagnosed ectopic salivary glands of the vocal cord.

Conclusion: It is necessary to consider the possibility of ectopic salivary glands as mass lesions of the vocal cords. Surgical resection is required and long-term follow-up is necessary after surgery.

简介唾液腺异位在声带中很少见,在英文文献中仅有两例报道。据我们所知,这是第三例此类异常病例。病例介绍。一名 78 岁的男性患者两年前因声音嘶哑来我科就诊。他没有咳嗽或喉咙痛等其他症状。他没有吸烟史。喉内窥镜检查发现他的右声带前部有一个光滑的肿块。我们在全身麻醉下进行了手术,切除了息肉,改善了声音嘶哑。组织病理标本显示为唾液腺组织。我们诊断为声带异位唾液腺:结论:有必要考虑异位唾液腺作为声带肿块病变的可能性。结论:有必要考虑异位涎腺作为声带肿块病变的可能性,需要进行手术切除,术后需要长期随访。
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引用次数: 0
Pleomorphic Adenoma of the Palate: Diagnostic and Surgical Strategy. 腭部多形腺瘤:诊断和手术策略。
IF 0.4 Q4 OTORHINOLARYNGOLOGY Pub Date : 2024-08-06 eCollection Date: 2024-01-01 DOI: 10.1155/2024/6400515
Ciré Ndiaye, Mame Sanou Diouf, Houra Ahmed, Arame Thiam, Ngoné Diaba Diop, Aminata Mbaye, Mamadou Woury Barry, Mame Diarra Bousso Ba

Pleomorphic adenoma is a benign tumor of the salivary glands. It develops preferentially in the parotid gland. The authors report a localization of a pleomorphic adenoma on the palate and discuss the value of CT scan in therapeutic strategy.

多形性腺瘤是唾液腺的一种良性肿瘤。它好发于腮腺。作者报告了上颚多形性腺瘤的定位,并讨论了 CT 扫描在治疗策略中的价值。
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引用次数: 0
Oral Rehabilitation for a Patient with Cocaine-Induced Midline Destructive Lesions. 可卡因导致的中线破坏性病变患者的口腔康复治疗。
IF 0.4 Q4 OTORHINOLARYNGOLOGY Pub Date : 2024-06-19 eCollection Date: 2024-01-01 DOI: 10.1155/2024/7109261
Antoine Berberi, Elie Azar

Background: Cocaine is the second most consumed drug worldwide, more than 0.4% of the global population, and has become a real public health problem in recent years. Its inhalation causes significant centrofacial lesions, grouped under the name cocaine-induced midline destructive lesion (CIMDL). These destructions are due to the conjunction of the vasoconstrictor, local prothrombogenic effects, and cytotoxic effects of cocaine. The ischemia produced by this substance is due to vasoconstriction that leads to nasal tissue necrosis and perforation of the nasal septum secondary to chondral necrosis. Case Presentation. A 36-year-old man, previously grappling with cocaine addiction, was hospitalized to undergo comprehensive clinical, microbiological, and radiological examinations because he was suffering from the emergence of crusts and ulceration in the nasal mucosa, accompanied by a palate perforation, a 39°C fever, and chills. Standard bacteriological culture was positive for coagulase-negative staphylococci and Escherichia coli, while mycological culture was positive for Candida tropicalis. The CT scan images of the sinuses confirmed the presence of palatal perforation and total destruction of the nasal septum, cartilaginous portion, maxillary sinus medial wall, lower and middle turbinates, and middle meatus. Nasal endoscopy revealed an exposition of the bony wall and displayed the exposition of the occipital bone's clivus. A diagnosis of CIMDL was confirmed. Antibiotic therapy was decided based on antibiogram results by the consulting microbiologist. Debridement of necrotic tissue was done by nasal endoscopy with local cleaning and was repetitive during the first week to maintain the best cleanliness possible. The patient was discharged with oro-nasal hygiene instructions and referred for prosthetic rehabilation. As for the cocaine addiction, the patient was in follow-up with a psychologist in a specialized centre.

Conclusion: The care is multidisciplinary. Psychological help and assistance are essential to guide patients to become cocaine free and to avoid a relapse. Weaning is a prerequisite for surgery. Rehabilitation of speech and swallowing is necessary. Many local flaps or micro-anastomoses are possible.

背景:可卡因是全球第二大消费毒品,占全球人口的 0.4%以上,近年来已成为一个真正的公共卫生问题。吸入可卡因会导致严重的面部中心病变,被称为可卡因诱发的中线破坏性病变(CIMDL)。这些破坏是由于可卡因的血管收缩效应、局部促血栓形成效应和细胞毒性效应共同作用的结果。这种物质造成的缺血是由于血管收缩导致鼻腔组织坏死和鼻中隔软骨坏死继发穿孔。病例介绍。一名 36 岁的男子曾因可卡因成瘾而苦恼不已,他因鼻粘膜出现结痂和溃疡,并伴有上颚穿孔、39°C 发烧和寒战而住院,接受了全面的临床、微生物学和放射学检查。标准细菌培养呈凝固酶阴性葡萄球菌和大肠杆菌阳性,霉菌培养呈热带念珠菌阳性。鼻窦 CT 扫描图像证实存在腭部穿孔,鼻中隔、软骨部分、上颌窦内侧壁、中下鼻甲和中鼻孔完全被毁。鼻内窥镜检查发现骨壁外露,并显示枕骨嵴外露。确诊为 CIMDL。根据微生物咨询专家的抗生素检查结果,决定采用抗生素治疗。通过鼻内窥镜对坏死组织进行了清创,并进行了局部清洁,在第一周内反复进行,以尽可能保持清洁。患者出院时接受了口鼻卫生指导,并被转诊至假体康复中心。至于可卡因成瘾问题,患者在一家专业中心接受了心理医生的随访:结论:护理是多学科的。心理帮助和援助对于指导患者戒除可卡因和避免复吸至关重要。断奶是手术的先决条件。语言和吞咽功能的康复是必要的。许多局部皮瓣或微型吻合术都是可行的。
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引用次数: 0
A Case of Sublingual Gland Hypertrophy in the Setting of Submandibular Gland Aplasia Presenting as a Neck Mass. 一例在颌下腺增生的情况下出现舌下腺肥大并表现为颈部肿块的病例。
IF 0.4 Q4 OTORHINOLARYNGOLOGY Pub Date : 2024-06-17 eCollection Date: 2024-01-01 DOI: 10.1155/2024/8610465
Colten Wolf, Richard Hubbell

Background: Absence or aplasia of the major salivary glands is an uncommon diagnosis and is often associated with other congenital abnormalities. Agenesis of a single submandibular gland, however, is an even more rare phenomenon and can be associated with hypertrophy of other salivary glands.

Methods: A 48-year-old female presented to the clinic with a left-sided neck mass below her mandible. Workup including a CT scan showed an absent left-sided submandibular gland and an enlarged sublingual gland protruding through the mylohyoid muscle.

Results: The patient underwent a transoral resection of the mass with subsequent resolution of the mass. The pathology returned as normal salivary gland tissue.

Conclusions: Sublingual gland hypertrophy is a very uncommon presentation for a patient with a neck mass. This situation can arise in the setting of submandibular gland aplasia and compensatory hypertrophy of other salivary glands.

背景:主要唾液腺缺失或增生是一种不常见的诊断,通常与其他先天性畸形有关。然而,单个颌下腺的缺失是一种更为罕见的现象,而且可能与其他唾液腺的肥大有关:一名 48 岁女性因下颌骨下方左侧颈部肿块就诊。包括 CT 扫描在内的检查结果显示,左侧颌下腺缺失,肿大的舌下腺通过舌骨肌突出:患者接受了经口肿块切除术,随后肿块消退。病理结果显示唾液腺组织正常:舌下腺肥大是颈部肿块患者中非常少见的一种表现。这种情况可能发生在颌下腺增生和其他唾液腺代偿性肥大的情况下。
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引用次数: 0
Ciliary Functional Analysis in Chronic Rhinosinusitis with Polyps after Multimodal Intervention: Oral Corticosteroid, Functional Endoscopic Sinus Surgery, and Omalizumab Injection 多模式干预后伴有息肉的慢性鼻窦炎患者的纤毛功能分析:口服皮质类固醇、功能性内窥镜鼻窦手术和奥马珠单抗注射液
IF 0.6 Pub Date : 2024-05-14 DOI: 10.1155/2024/5559001
L. Benchimol, Olivier Bouchain, N. Bricmont, R. Bonhiver, C. Kempeneers, Philippe Lefebvre, A. Poirrier
In her late 50 s, a woman with a medical history of endoscopic sinus surgery for chronic rhinosinusitis with nasal polyps (CRSwNP) experienced a relapse of nasal polyps, significantly impacting her breathing and sense of smell. She underwent a multifaceted treatment approach, including oral corticosteroids, functional endoscopic sinus surgery, and omalizumab injections. Digital high-speed videomicroscopy (DHSV) revealed only partial improvement in ciliary beat pattern and ciliary beat frequency with oral corticosteroid treatment, while significant improvement in these ciliary parameters was observed with omalizumab injections. Furthermore, administration of omalizumab resulted in a decrease in her SNOT-22 (Sinonasal Outcome Test 22) score. Notably, this case report represents the first study investigating ciliary function using DHSV in a patient treated with omalizumab.
一位 50 多岁的妇女曾因慢性鼻炎伴鼻息肉(CRSwNP)接受过内窥镜鼻窦手术治疗,后来鼻息肉复发,严重影响了她的呼吸和嗅觉。她接受了多方面的治疗,包括口服皮质类固醇、功能性内窥镜鼻窦手术和奥马珠单抗注射。数字高速视频显微镜(DHSV)显示,口服皮质类固醇治疗只能部分改善睫状肌搏动模式和睫状肌搏动频率,而注射奥马珠单抗后,这些睫状肌参数有了明显改善。此外,注射奥马珠单抗还降低了她的 SNOT-22(Sinonasal Outcome Test 22)评分。值得注意的是,本病例报告是利用 DHSV 对接受奥马珠单抗治疗的患者的睫状体功能进行的首次研究。
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引用次数: 0
Challenges in the Management of Massive Carotid Body Tumor. 治疗巨大颈动脉体瘤的挑战。
IF 0.6 Pub Date : 2024-04-29 eCollection Date: 2024-01-01 DOI: 10.1155/2024/9963521
Oluwapelumi Olusoga-Peters, Moses Ayodele Akinola, John Ifeanyi Nwadiokwu, Florence Oguntade

The carotid body paraganglioma is a rare benign neoplasm arising from the chemoreceptor cells of the carotid bulb. The carotid body has the largest collection of paraganglia in the head and neck with 60-70% of head and neck paraganglioma. Paraganglia are clusters of cells originating from the neural crest with histological and cytochemical characteristics of neuroendocrine cells. It is mostly asymptomatic in early presentation but become symptomatic and difficult to manage when the tumor is large. We present a case of a 26-year-old male who presented with a painless, pulsatile, progressively increasing left lateral neck swelling of 5 years duration with Shamblin IIIa. The diagnosis of the tumor was confirmed based on clinical features, histology, and radiological findings. We had difficult surgical dissection of the tumor with neurovascular damage.

颈动脉体副神经节瘤是一种罕见的良性肿瘤,产生于颈动脉球的化学感受器细胞。颈动脉体是头颈部副神经节最多的部位,占头颈部副神经节瘤的 60-70%。副神经节是起源于神经嵴的细胞团,具有神经内分泌细胞的组织学和细胞化学特征。早期多无症状,但肿瘤较大时会出现症状,且难以处理。我们报告了一例 26 岁男性的病例,他出现无痛性、搏动性、逐渐增大的左侧颈部肿物,病程 5 年,伴有 Shamblin IIIa。根据临床特征、组织学和放射学检查结果确诊为肿瘤。我们对肿瘤进行了困难的手术切除,并造成了神经血管损伤。
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引用次数: 0
SDHAF2-Linked Metastatic Paraganglioma: A Case Report with Implications for Counseling and Follow-Up of Pathogenic SDHAF2 Variant Carriers SDHAF2相关转移性副神经节瘤:病例报告及对致病性 SDHAF2 变异携带者的咨询和随访的启示
IF 0.6 Pub Date : 2024-03-20 DOI: 10.1155/2024/2111531
Monique A. M. de Jong, E. Corssmit, J. C. Jansen, T. Potjer, J. Bayley, E. Hensen
Head and neck paragangliomas are slow growing and highly vascular neuroendocrine tumors. It is currently assumed that SDHAF2 variants exclusively cause benign and often multicentric head and neck paragangliomas. Here, we present a patient diagnosed with multiple SDHAF2-linked head and neck paragangliomas who in addition developed paraganglioma metastases to the lung and spine and a primary or metastatic paraganglioma in the head of the pancreas. During the course of the disease, a range of management strategies were deployed for the different head and neck tumors, including total resections, partial resections, and active surveillance. After identification of the paraganglioma metastases, the patient was treated with lanreotide after which the disease remained stable during the 27 months of follow-up.
头颈部副神经节瘤是一种生长缓慢、血管丰富的神经内分泌肿瘤。目前认为,SDHAF2 变体是导致头颈部副神经节瘤的唯一良性因素,而且往往是多中心性的。在这里,我们介绍了一名被诊断患有多个与 SDHAF2 相关的头颈部副神经节瘤的患者,该患者还出现了肺部和脊柱副神经节瘤转移以及胰腺头部原发性或转移性副神经节瘤。在病程中,针对不同的头颈部肿瘤采取了一系列治疗策略,包括全部切除、部分切除和积极监测。在确定副神经节瘤转移后,患者接受了兰瑞奥肽治疗,之后在27个月的随访期间病情保持稳定。
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引用次数: 0
Primary Cervical Extraosseous Ewing's Sarcoma Originated from the Sternocleidomastoid Muscle: A Case Report and Review of the Literature. 起源于胸锁乳突肌的原发性颈椎骨外尤文氏肉瘤:病例报告和文献综述。
IF 0.6 Pub Date : 2024-02-22 eCollection Date: 2024-01-01 DOI: 10.1155/2024/8867131
Sasa Jakovljevic, Nenad Arsovic, Zoran Dudvarski, Nemanja Radivojevic, Katarina Jovanovic, Neda Mladenovic, Snezana Babac

Extraosseous Ewing's sarcoma is extremely rare in the soft tissues of the neck, especially in the sternocleidomastoid muscle. It usually manifests clinically as a rapidly growing mass that shows great potential for local spread. The aim of this paper is to present a rare case of еxtraosseous Ewing's sarcoma in the sternocleidomastoid muscle. To the best of our knowledge, this is the first case of extraskeletal Ewing's sarcoma at this location. The patient was admitted to our clinic because of a neck tumefaction. The computerized tomography finding showed a tumor mass, most of which was in the V region of the neck, measuring 40 × 27 × 35 mm. Pathohistological and immunohistochemical findings showed that it was Ewing's sarcoma. Unfortunately, the patient passed away nine months after the initial diagnosis. Extraosseous Ewing sarcoma is a rare, fast-growing malignant tumor manifesting histomorphological similarities to bone Ewing's sarcoma. Most reports state that extraosseous Ewing sarcoma has a worse prognosis than skeletal. Extraosseous Ewing sarcoma should be borne in mind in the differential diagnosis of soft tissue tumors of the neck.

骨外尤文氏肉瘤在颈部软组织,尤其是胸锁乳突肌中极为罕见。其临床表现通常为迅速生长的肿块,极有可能发生局部扩散。本文旨在介绍一例罕见的胸锁乳突肌骨外尤文氏肉瘤病例。据我们所知,这是第一例发生在该部位的骨外尤文氏肉瘤。患者因颈部肿瘤入院。计算机断层扫描结果显示,肿瘤肿块大部分位于颈部 V 区,大小为 40 × 27 × 35 毫米。病理组织学和免疫组化结果显示,这是尤文氏肉瘤。不幸的是,患者在确诊九个月后去世。骨外尤文肉瘤是一种罕见的快速生长恶性肿瘤,其组织形态与骨尤文肉瘤相似。大多数报告指出,骨外尤文肉瘤的预后比骨骼型尤文肉瘤差。在鉴别诊断颈部软组织肿瘤时应注意骨外尤文肉瘤。
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引用次数: 0
Cerebellar Compression by Giant Extracanalicular Osteoma with Central Cholesterol Granuloma 伴有中央胆固醇肉芽肿的巨大颅外骨瘤压迫小脑
IF 0.6 Pub Date : 2023-12-15 DOI: 10.1155/2023/6652012
Caroline F. Smith, Conner J. Massey, Scott E. Mann
Temporal bone osteomas comprise 0.1–1% of benign tumors involving the skull, the majority of which arise in the external auditory canal. More rarely, they can arise from the mastoid portion of the temporal bone. These generally present as a slow growing skull base lesion that can cause cosmetic deformity, headache, and/or hearing loss. Here, we report a case of extracanalicular mastoid osteoma uniquely presenting with posterior fossa and cerebellar compression with associated dizziness and imbalance.
颞骨骨瘤占累及颅骨的良性肿瘤的 0.1-1%,其中大部分发生在外耳道。更罕见的是,它们可能来自颞骨的乳突部分。这些肿瘤通常表现为生长缓慢的颅底病变,可导致外观畸形、头痛和/或听力损失。在此,我们报告了一例独特的乳突骨瘤病例,患者表现为后窝和小脑受压,并伴有头晕和失衡。
{"title":"Cerebellar Compression by Giant Extracanalicular Osteoma with Central Cholesterol Granuloma","authors":"Caroline F. Smith, Conner J. Massey, Scott E. Mann","doi":"10.1155/2023/6652012","DOIUrl":"https://doi.org/10.1155/2023/6652012","url":null,"abstract":"Temporal bone osteomas comprise 0.1–1% of benign tumors involving the skull, the majority of which arise in the external auditory canal. More rarely, they can arise from the mastoid portion of the temporal bone. These generally present as a slow growing skull base lesion that can cause cosmetic deformity, headache, and/or hearing loss. Here, we report a case of extracanalicular mastoid osteoma uniquely presenting with posterior fossa and cerebellar compression with associated dizziness and imbalance.","PeriodicalId":45872,"journal":{"name":"Case Reports in Otolaryngology","volume":null,"pages":null},"PeriodicalIF":0.6,"publicationDate":"2023-12-15","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"138998266","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
引用次数: 0
Respiratory Epithelial Adenomatoid Hamartoma: An Uncommon Differential of Nasopharyngeal Tumor. 呼吸道上皮腺瘤样脂肪瘤:一种不常见的鼻咽肿瘤鉴别诊断。
IF 0.6 Pub Date : 2023-11-30 eCollection Date: 2023-01-01 DOI: 10.1155/2023/9942293
Taiwo Olufemi Solaja, Kenechukwu Chinemelum Uche-Okonkwo, Moses Ayodele Akinola, John Ifeanyi Nwadiokwu

Respiratory epithelial adenomatoid hamartoma (REAH) is an uncommon tumor-like lesion that has been reported within the nose, paranasal sinuses, and less frequently in the nasopharynx. While it is believed to be benign, its clinical presentation, radiological characteristics, and microscopic features may closely mimic more aggressive tumors of the upper respiratory tract, potentially leading to needless life-altering treatment. Prior to now, there had been no reported cases of this lesion in West Africa. We present a 35-year-old male with persistent bilateral nasal obstruction, difficulty with swallowing, and bilateral reduction in hearing, whose CT findings were highly suggestive of a nasopharyngeal tumor, but upon biopsy and histology showed features most consistent with REAH. Surgery completely alleviated his symptoms with no clinical evidence of recurrence after a 1-year follow-up period.

呼吸道上皮腺瘤样火腿肠瘤(REAH)是一种不常见的肿瘤样病变,在鼻腔、鼻旁窦和鼻咽部均有报道。虽然它被认为是良性的,但其临床表现、放射学特征和显微特征可能与上呼吸道中更具侵袭性的肿瘤非常相似,有可能导致不必要的改变生命的治疗。在此之前,西非还没有关于这种病变的病例报道。我们介绍了一名 35 岁的男性患者,他患有持续性双侧鼻腔阻塞、吞咽困难和双侧听力下降,CT 检查结果高度提示鼻咽肿瘤,但活检和组织学检查显示其特征与 REAH 最为一致。手术完全缓解了他的症状,随访一年后也没有发现复发的临床证据。
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引用次数: 0
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Case Reports in Otolaryngology
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