Pub Date : 2024-09-26DOI: 10.1016/j.radcr.2024.09.022
Intestinal volvulus is a pathological condition that can lead to bowel obstruction and intestinal ischemia, and is therefore potentially fatal in severe cases. Patients' symptoms are often nonspecific: volvulus most frequently presents as an acute abdomen, but vague symptoms such as abdominal pain and distension, nausea and vomiting are common. In this scenario, the gold standard for diagnosis is contrast-enhanced computed tomography, which allows a timely assessment. However, in this article we present a rare case of a small bowel volvulus associated with a sigmoid volvulus in which the patient presented to the emergency department with respiratory symptoms.
{"title":"An unusual case of small bowel and sigmoid volvuli presenting with dyspnea","authors":"","doi":"10.1016/j.radcr.2024.09.022","DOIUrl":"10.1016/j.radcr.2024.09.022","url":null,"abstract":"<div><div>Intestinal volvulus is a pathological condition that can lead to bowel obstruction and intestinal ischemia, and is therefore potentially fatal in severe cases. Patients' symptoms are often nonspecific: volvulus most frequently presents as an acute abdomen, but vague symptoms such as abdominal pain and distension, nausea and vomiting are common. In this scenario, the gold standard for diagnosis is contrast-enhanced computed tomography, which allows a timely assessment. However, in this article we present a rare case of a small bowel volvulus associated with a sigmoid volvulus in which the patient presented to the emergency department with respiratory symptoms.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-26","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142322666","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-26DOI: 10.1016/j.radcr.2024.09.013
The co-infection of cutaneous cytomegalovirus (CMV) and varicella-zoster virus (VZV) is a rare occurrence, particularly in the context of Good's syndrome (GS). This report presents a unique case of a 56-year-old man with GS, characterized by a thymoma, who developed cutaneous CMV and VZV co-infections. We discuss the clinical characteristics, diagnostic process, and treatment of this uncommon manifestation. A 56-year-old man with a mediastinal mass identified as thymoma type A and pleural metastasis, presented with a three-week progressive, painful generalized skin lesions on his face, trunk, and extremities. Upon further examination, multiple extensive vesicles with reddened bases were distributed throughout all regions of his body, some exhibited hemorrhagic characteristics. The histopathologic assessment indicated a herpes virus infection and leukocytoclastic vasculitis. Additionally, Immunohistochemistry staining for CMV highlighted infected endothelial cells. The patient was diagnosed with disseminated cutaneous co-infection of CMV and VZV in the context of Good's syndrome. The patient responded well to a treatment regimen combining intravenous immunoglobulin (IVIG) and ganciclovir therapy, leading to the complete resolution of skin lesions. He was recommended prophylactic treatment and showed significant improvement upon follow-up, ultimately being discharged in a favorable clinical condition. By gaining a better understanding of this condition, healthcare professionals can improve their ability to recognize and treat Good's syndrome effectively. Early identification and effective treatment have a crucial role in enhancing the prognosis.
{"title":"Unusual presentation of cytomegalovirus and varicella-zoster virus infection in a patient with good's syndrome: A case report","authors":"","doi":"10.1016/j.radcr.2024.09.013","DOIUrl":"10.1016/j.radcr.2024.09.013","url":null,"abstract":"<div><div>The co-infection of cutaneous cytomegalovirus (CMV) and varicella-zoster virus (VZV) is a rare occurrence, particularly in the context of Good's syndrome (GS). This report presents a unique case of a 56-year-old man with GS, characterized by a thymoma, who developed cutaneous CMV and VZV co-infections. We discuss the clinical characteristics, diagnostic process, and treatment of this uncommon manifestation. A 56-year-old man with a mediastinal mass identified as thymoma type A and pleural metastasis, presented with a three-week progressive, painful generalized skin lesions on his face, trunk, and extremities. Upon further examination, multiple extensive vesicles with reddened bases were distributed throughout all regions of his body, some exhibited hemorrhagic characteristics. The histopathologic assessment indicated a herpes virus infection and leukocytoclastic vasculitis. Additionally, Immunohistochemistry staining for CMV highlighted infected endothelial cells. The patient was diagnosed with disseminated cutaneous co-infection of CMV and VZV in the context of Good's syndrome. The patient responded well to a treatment regimen combining intravenous immunoglobulin (IVIG) and ganciclovir therapy, leading to the complete resolution of skin lesions. He was recommended prophylactic treatment and showed significant improvement upon follow-up, ultimately being discharged in a favorable clinical condition. By gaining a better understanding of this condition, healthcare professionals can improve their ability to recognize and treat Good's syndrome effectively. Early identification and effective treatment have a crucial role in enhancing the prognosis.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-26","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142322665","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-26DOI: 10.1016/j.radcr.2024.09.055
The management of B3 breast lesions using vacuum-assisted excision (VAE) is gaining increasing traction in clinical practice. However, it is infrequently reported in the literature how this technique may affect long-term imaging appearances. We present a challenging case in which the previous VAE site displayed a mass-like appearance that mimicked breast cancer. The purpose of this case report is to share our experience and illustrate the ultrasound and mammographic characteristics of the residual cavity after VAE, in order to contribute to expanding knowledge regarding radiological imaging post-VAE, which is currently still limited.
{"title":"Diagnostic pitfall in radiological imaging after vacuum-assisted excision of B3 breast lesion: A case report","authors":"","doi":"10.1016/j.radcr.2024.09.055","DOIUrl":"10.1016/j.radcr.2024.09.055","url":null,"abstract":"<div><div>The management of B3 breast lesions using vacuum-assisted excision (VAE) is gaining increasing traction in clinical practice. However, it is infrequently reported in the literature how this technique may affect long-term imaging appearances. We present a challenging case in which the previous VAE site displayed a mass-like appearance that mimicked breast cancer. The purpose of this case report is to share our experience and illustrate the ultrasound and mammographic characteristics of the residual cavity after VAE, in order to contribute to expanding knowledge regarding radiological imaging post-VAE, which is currently still limited.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-26","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142322663","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-26DOI: 10.1016/j.radcr.2024.09.117
Coronary artery fistulas (CAF) are rare abnormalities involving a connection between a coronary artery and an adjacent vessel or heart chamber. Here we discuss the case of a 47-year-old male patient who had multiple gunshot wounds (GSWs) to the chest and abdomen, suffering a through and through bullet wound to the heart from the left ventricle (LV) through the left anterior descending (LAD) coronary artery and exiting from the right ventricle (RV). At the time of his hospitalization, he underwent a non-ECG gated trauma CT scan and subsequent cardiac catheterization that showed patient has a CAF between the LAD and RVOT. Roughly 3 years after his injury, the patient had an ECG-gated coronary CT scan showing the CAF is still present. The patient is now experiencing symptoms of heart failure with suspected worsening of shunt flow from the fistula. This case sheds light on CAFs, their presentation and potential complications to raise awareness for clinicians and radiologists.
{"title":"Traumatic injury of the left anterior descending coronary artery with fistula to the right ventricular outflow tract postgunshot wound","authors":"","doi":"10.1016/j.radcr.2024.09.117","DOIUrl":"10.1016/j.radcr.2024.09.117","url":null,"abstract":"<div><div>Coronary artery fistulas (CAF) are rare abnormalities involving a connection between a coronary artery and an adjacent vessel or heart chamber. Here we discuss the case of a 47-year-old male patient who had multiple gunshot wounds (GSWs) to the chest and abdomen, suffering a through and through bullet wound to the heart from the left ventricle (LV) through the left anterior descending (LAD) coronary artery and exiting from the right ventricle (RV). At the time of his hospitalization, he underwent a non-ECG gated trauma CT scan and subsequent cardiac catheterization that showed patient has a CAF between the LAD and RVOT. Roughly 3 years after his injury, the patient had an ECG-gated coronary CT scan showing the CAF is still present. The patient is now experiencing symptoms of heart failure with suspected worsening of shunt flow from the fistula. This case sheds light on CAFs, their presentation and potential complications to raise awareness for clinicians and radiologists.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-26","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142322664","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-26DOI: 10.1016/j.radcr.2024.08.137
Rudimentary uterine horn pregnancy is rare, with a reported incidence of 1 in 76,000 to 1 in 150,000. This report aims to advance knowledge regarding this rare condition, importance of MRI imaging in characterizing congenital uterine anomalies and the feasibility of a total laparoscopic management approach. A 26 year old female presented with new onset abdominal pain at 6 weeks gestation. Ultrasound imaging initially suggested that the pregnancy was located within a unicornuate uterus. However further imaging (ultrasound and MRI) instead located the pregnancy within a noncommunicating right-sided rudimentary uterine horn, with a left-sided unicornuate uterus. This uterine anomaly was newly diagnosed in early pregnancy and required a multidisciplinary approach to determine optimal management. A total laparoscopic approach was successfully used to excise the right uterine horn and fallopian tube to prevent recurrence and future complications including tubal ectopic pregnancy.
{"title":"Early first trimester diagnosis and total laparoscopic management of rudimentary uterine horn pregnancy","authors":"","doi":"10.1016/j.radcr.2024.08.137","DOIUrl":"10.1016/j.radcr.2024.08.137","url":null,"abstract":"<div><div>Rudimentary uterine horn pregnancy is rare, with a reported incidence of 1 in 76,000 to 1 in 150,000. This report aims to advance knowledge regarding this rare condition, importance of MRI imaging in characterizing congenital uterine anomalies and the feasibility of a total laparoscopic management approach. A 26 year old female presented with new onset abdominal pain at 6 weeks gestation. Ultrasound imaging initially suggested that the pregnancy was located within a unicornuate uterus. However further imaging (ultrasound and MRI) instead located the pregnancy within a noncommunicating right-sided rudimentary uterine horn, with a left-sided unicornuate uterus. This uterine anomaly was newly diagnosed in early pregnancy and required a multidisciplinary approach to determine optimal management. A total laparoscopic approach was successfully used to excise the right uterine horn and fallopian tube to prevent recurrence and future complications including tubal ectopic pregnancy.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-26","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142322667","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-25DOI: 10.1016/j.radcr.2024.09.047
Falciform ligament is a double fold of the peritoneum which has fat attached to it. The torsion of this fat leads to appendigitis which is a rare cause of acute severe epigastric pain. A 7-year-old boy presented with severe epigastric pain and vomiting of 3 days duration with associated epigastric tenderness. Ultrasound showed echogenic mass lesion adjacent to falciform ligament without color flow with associated thickening of the ligament which resolved after 01 week on follow up visit. Falciform ligament appendigitis is a rare cause of epigastric pain in the general spopulation and in pediatrics age group which should be considered in appropriate clinical setup. Early suggestion of falciform ligament appendigitis by a radiologist can help to avoid unnecessary surgeries as the clinical picture of this benign process overlaps with other surgical emergencies.
{"title":"An uncommon cause of epigastric pain in a child: falciform ligament appendigitis","authors":"","doi":"10.1016/j.radcr.2024.09.047","DOIUrl":"10.1016/j.radcr.2024.09.047","url":null,"abstract":"<div><div>Falciform ligament is a double fold of the peritoneum which has fat attached to it. The torsion of this fat leads to appendigitis which is a rare cause of acute severe epigastric pain. A 7-year-old boy presented with severe epigastric pain and vomiting of 3 days duration with associated epigastric tenderness. Ultrasound showed echogenic mass lesion adjacent to falciform ligament without color flow with associated thickening of the ligament which resolved after 01 week on follow up visit. Falciform ligament appendigitis is a rare cause of epigastric pain in the general spopulation and in pediatrics age group which should be considered in appropriate clinical setup. Early suggestion of falciform ligament appendigitis by a radiologist can help to avoid unnecessary surgeries as the clinical picture of this benign process overlaps with other surgical emergencies.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-25","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142318657","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-25DOI: 10.1016/j.radcr.2024.09.107
Mycobacterium has presented public health challenges since its inception, primarily affecting developing nations. Much less is known about M. bovis, a member of the mycobacterium family more frequently affecting zoonotic species. Infections postaortic aneurysm repair are rare, and few cases have reported infection secondary to the lesser-known mycobacterium member, M. bovis. Here, we present a case of aortic graft infection status-post aortic aneurysm repair secondary to M. bovis. We highlight the essential role multi-modal radiographic imaging played in establishing this diagnosis.
{"title":"Mycobacterium bovis: An unusual cause of aortic graft infection","authors":"","doi":"10.1016/j.radcr.2024.09.107","DOIUrl":"10.1016/j.radcr.2024.09.107","url":null,"abstract":"<div><div><em>Mycobacterium</em> has presented public health challenges since its inception, primarily affecting developing nations. Much less is known about <em>M. bovis</em>, a member of the mycobacterium family more frequently affecting zoonotic species. Infections postaortic aneurysm repair are rare, and few cases have reported infection secondary to the lesser-known mycobacterium member, <em>M. bovis.</em> Here, we present a case of aortic graft infection status-post aortic aneurysm repair secondary to <em>M. bovis.</em> We highlight the essential role multi-modal radiographic imaging played in establishing this diagnosis.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-25","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142318655","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-25DOI: 10.1016/j.radcr.2024.09.116
Adrenocortical tumors in children and adolescents are rare and aggressive, accounting for only 0.2% of pediatric cancers, with most cases associated with Li-Fraumeni syndrome. The most common manifestation is virilization due to androgen excess. Imaging techniques are crucial in the diagnosis and management of pediatric adrenocortical carcinoma. CT and MRI are essential for differentiating between benign and malignant lesions and assessing tumor characteristics and extent. Correlating imaging findings with clinical and histopathological data is vital for optimal diagnosis and treatment, underscoring the need for a multidisciplinary approach to managing these rare but aggressive neoplasms. This report presents the case of a previously healthy 2-year-old boy who exhibited virilization symptoms and was diagnosed with adrenocortical carcinoma.
{"title":"Adrenocortical neoplasm in a 2-year-old child: Clinical approach and diagnostic imaging","authors":"","doi":"10.1016/j.radcr.2024.09.116","DOIUrl":"10.1016/j.radcr.2024.09.116","url":null,"abstract":"<div><div>Adrenocortical tumors in children and adolescents are rare and aggressive, accounting for only 0.2% of pediatric cancers, with most cases associated with Li-Fraumeni syndrome. The most common manifestation is virilization due to androgen excess. Imaging techniques are crucial in the diagnosis and management of pediatric adrenocortical carcinoma. CT and MRI are essential for differentiating between benign and malignant lesions and assessing tumor characteristics and extent. Correlating imaging findings with clinical and histopathological data is vital for optimal diagnosis and treatment, underscoring the need for a multidisciplinary approach to managing these rare but aggressive neoplasms. This report presents the case of a previously healthy 2-year-old boy who exhibited virilization symptoms and was diagnosed with adrenocortical carcinoma.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-25","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142318656","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-25DOI: 10.1016/j.radcr.2024.09.077
Castleman's disease (CD) is a rare, benign nonclonal lymphoproliferative disorder with an unclear etiology, presenting significant diagnostic challenges due to its nonspecific features. CD is categorized into unicentric (UCD) and multicentric (MCD) types, with MCD further divided into HHV-8-associated and idiopathic (iMCD) forms. Clinical manifestations include fever, weight loss, night sweats, and organomegaly, with specific symptoms depending on the subtype. Diagnostic criteria for CD involve a combination of major criteria-histopathologic examination and minor criteria. Imaging techniques, including CT, MRI, and PET-CT, play a crucial role in diagnosis, staging, and differentiation from other diseases. This paper discusses the pathophysiology, clinical features, diagnostic criteria, and imaging findings of CD, illustrated by a case of a patient with renal disease with incidentally detected a right cardiophrenic mass. The case highlights the importance of comprehensive imaging and clinical evaluation in managing CD.
卡斯特曼病(CD)是一种罕见的良性非克隆性淋巴细胞增生性疾病,病因不清,由于其非特异性特征,给诊断带来了巨大挑战。CD分为单中心型(UCD)和多中心型(MCD),其中MCD又分为HHV-8相关型和特发性(iMCD)型。临床表现包括发热、体重减轻、盗汗和器官肿大,具体症状取决于亚型。CD 的诊断标准包括主要标准(组织病理学检查)和次要标准。包括 CT、MRI 和 PET-CT 在内的影像学技术在诊断、分期和与其他疾病鉴别方面起着至关重要的作用。本文讨论了 CD 的病理生理学、临床特征、诊断标准和影像学发现,并以一例偶然发现右心房肿块的肾病患者为例进行说明。该病例强调了综合影像学和临床评估在治疗 CD 方面的重要性。
{"title":"Diaphragmatic Castleman's disease: A rare lymphoproliferative disorder: Clinical and radiological perspectives","authors":"","doi":"10.1016/j.radcr.2024.09.077","DOIUrl":"10.1016/j.radcr.2024.09.077","url":null,"abstract":"<div><div>Castleman's disease (CD) is a rare, benign nonclonal lymphoproliferative disorder with an unclear etiology, presenting significant diagnostic challenges due to its nonspecific features. CD is categorized into unicentric (UCD) and multicentric (MCD) types, with MCD further divided into HHV-8-associated and idiopathic (iMCD) forms. Clinical manifestations include fever, weight loss, night sweats, and organomegaly, with specific symptoms depending on the subtype. Diagnostic criteria for CD involve a combination of major criteria-histopathologic examination and minor criteria. Imaging techniques, including CT, MRI, and PET-CT, play a crucial role in diagnosis, staging, and differentiation from other diseases. This paper discusses the pathophysiology, clinical features, diagnostic criteria, and imaging findings of CD, illustrated by a case of a patient with renal disease with incidentally detected a right cardiophrenic mass. The case highlights the importance of comprehensive imaging and clinical evaluation in managing CD.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-25","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142318652","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}
Pub Date : 2024-09-25DOI: 10.1016/j.radcr.2024.08.056
Recorded findings of Herlyn-Werner-Wunderlich Syndrome (HWWS) remain sparse due to low statistical incidence. Ours is also the first known case to present with an ectopic urethral opening, an even rarer complication. A 27-year-old nulliparous woman presented with complaints of cyclical hematuria, and burning micturition with intermittent episodes of urinary retention suprapubic and pelvic pain. After extensive radiological examination, the MRI findings concluded the presence of a uterine didelphys with 2 cervixes and vaginal duplication marked by the compression of the left hemivagina and dilation of the right hemivagina, pointing towards HWWS. The case strongly suggests that the presence of an ectopic urethral opening may be the cause of urinary incontinence and discomfort in an otherwise asymptomatic patient of HWWS.
{"title":"Ectopic urethral opening in herlyn-werner-wunderlich syndrome: A rare finding","authors":"","doi":"10.1016/j.radcr.2024.08.056","DOIUrl":"10.1016/j.radcr.2024.08.056","url":null,"abstract":"<div><div>Recorded findings of Herlyn-Werner-Wunderlich Syndrome (HWWS) remain sparse due to low statistical incidence. Ours is also the first known case to present with an ectopic urethral opening, an even rarer complication. A 27-year-old nulliparous woman presented with complaints of cyclical hematuria, and burning micturition with intermittent episodes of urinary retention suprapubic and pelvic pain. After extensive radiological examination, the MRI findings concluded the presence of a uterine didelphys with 2 cervixes and vaginal duplication marked by the compression of the left hemivagina and dilation of the right hemivagina, pointing towards HWWS. The case strongly suggests that the presence of an ectopic urethral opening may be the cause of urinary incontinence and discomfort in an otherwise asymptomatic patient of HWWS.</div></div>","PeriodicalId":53472,"journal":{"name":"Radiology Case Reports","volume":null,"pages":null},"PeriodicalIF":0.0,"publicationDate":"2024-09-25","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":null,"resultStr":null,"platform":"Semanticscholar","paperid":"142318659","PeriodicalName":null,"FirstCategoryId":null,"ListUrlMain":null,"RegionNum":0,"RegionCategory":"","ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":"OA","EPubDate":null,"PubModel":null,"JCR":null,"JCRName":null,"Score":null,"Total":0}